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伴有皮质下囊肿的巨脑性白质脑病:与白质囊性变性相关的皮质下弥漫性白质脑病。

Megalencephalic leucoencephalopathy with subcortical cysts: subcortical diffuse leucoencephalopathy associated with white matter cystic degeneration.

作者信息

Dash Prafulla Kumar, Raj Dinesh Harvey, Sahu Hrushikesh

机构信息

Department of Radiodiagnosis, CMIIL-SCB Medical MRI Centre, Cuttack, Odisha, India.

Department of Radiodiagnosis, SCB Medical College, Cuttack, Odisha, India.

出版信息

BMJ Case Rep. 2015 Sep 21;2015:bcr2015211921. doi: 10.1136/bcr-2015-211921.

Abstract

Megalencephalic leucoencephalopathy with subcortical cysts (MLC) is a diffuse subcortical leucoencephalopathy with cystic white matter degeneration. Patients with MLC present with macrocephaly at the first year of life, and neurological abnormalities such as motor deterioration, ataxia, spasticity and cognitive defects progress later. MLC is caused by mutations in the gene MLC1, which encodes a novel protein, MLC1. There is no specific treatment for MLC. Management is based on physiotherapy procedures, psychomotor stimulation and treatment of seizures. We report a case of a 1-year-old boy with a normal birth and developmental history, presenting with progressive increase of head size; on further evaluation with CT and MRI of the brain, the child was diagnosed as MLC.

摘要

巨脑回合并皮质下囊肿性白质脑病(MLC)是一种伴有囊性白质变性的弥漫性皮质下白质脑病。MLC患者在出生后第一年出现巨头畸形,随后出现运动功能恶化、共济失调、痉挛和认知缺陷等神经功能异常。MLC由MLC1基因突变引起,该基因编码一种新型蛋白质MLC1。目前尚无针对MLC的特异性治疗方法。治疗主要基于物理治疗、心理运动刺激和癫痫治疗。我们报告一例1岁男童,出生及发育史正常,出现头围逐渐增大;经头颅CT和MRI进一步评估,该患儿被诊断为MLC。

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本文引用的文献

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Indian Agarwal megalencephalic leukodystrophy with cysts is caused by a common MLC1 mutation.
Neurology. 2004 Mar 23;62(6):878-82. doi: 10.1212/01.wnl.0000115106.88813.5b.

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