Burkhardt Ralph, Kirsten Holger, Beutner Frank, Holdt Lesca M, Gross Arnd, Teren Andrej, Tönjes Anke, Becker Susen, Krohn Knut, Kovacs Peter, Stumvoll Michael, Teupser Daniel, Thiery Joachim, Ceglarek Uta, Scholz Markus
LIFE Leipzig Research Center for Civilization Diseases, University of Leipzig, Leipzig Germany; Institute of Laboratory Medicine, Clinical Chemistry and Molecular Diagnostics, University Hospital Leipzig, Leipzig, Germany.
LIFE Leipzig Research Center for Civilization Diseases, University of Leipzig, Leipzig Germany; Institute for Medical Informatics, Statistics and Epidemiology, University of Leipzig, Leipzig, Germany; Department for Cell Therapy, Fraunhofer Institute for Cell Therapy and Immunology, Leipzig, Germany.
PLoS Genet. 2015 Sep 24;11(9):e1005510. doi: 10.1371/journal.pgen.1005510. eCollection 2015 Sep.
Profiling amino acids and acylcarnitines in whole blood spots is a powerful tool in the laboratory diagnosis of several inborn errors of metabolism. Emerging data suggests that altered blood levels of amino acids and acylcarnitines are also associated with common metabolic diseases in adults. Thus, the identification of common genetic determinants for blood metabolites might shed light on pathways contributing to human physiology and common diseases. We applied a targeted mass-spectrometry-based method to analyze whole blood concentrations of 96 amino acids, acylcarnitines and pathway associated metabolite ratios in a Central European cohort of 2,107 adults and performed genome-wide association (GWA) to identify genetic modifiers of metabolite concentrations. We discovered and replicated six novel loci associated with blood levels of total acylcarnitine, arginine (both on chromosome 6; rs12210538, rs17657775), propionylcarnitine (chromosome 10; rs12779637), 2-hydroxyisovalerylcarnitine (chromosome 21; rs1571700), stearoylcarnitine (chromosome 1; rs3811444), and aspartic acid traits (chromosome 8; rs750472). Based on an integrative analysis of expression quantitative trait loci in blood mononuclear cells and correlations between gene expressions and metabolite levels, we provide evidence for putative causative genes: SLC22A16 for total acylcarnitines, ARG1 for arginine, HLCS for 2-hydroxyisovalerylcarnitine, JAM3 for stearoylcarnitine via a trans-effect at chromosome 1, and PPP1R16A for aspartic acid traits. Further, we report replication and provide additional functional evidence for ten loci that have previously been published for metabolites measured in plasma, serum or urine. In conclusion, our integrative analysis of SNP, gene-expression and metabolite data points to novel genetic factors that may be involved in the regulation of human metabolism. At several loci, we provide evidence for metabolite regulation via gene-expression and observed overlaps with GWAS loci for common diseases. These results form a strong rationale for subsequent functional and disease-related studies.
分析全血斑中的氨基酸和酰基肉碱是实验室诊断多种先天性代谢缺陷的有力工具。新出现的数据表明,成人血液中氨基酸和酰基肉碱水平的改变也与常见代谢疾病有关。因此,确定血液代谢物的常见遗传决定因素可能有助于揭示影响人类生理和常见疾病的途径。我们应用基于靶向质谱的方法,分析了2107名中欧成年人队列中96种氨基酸、酰基肉碱和途径相关代谢物比率的全血浓度,并进行了全基因组关联研究(GWA)以确定代谢物浓度的遗传修饰因子。我们发现并重复验证了6个与总酰基肉碱、精氨酸(均位于6号染色体;rs12210538、rs17657775)、丙酰肉碱(10号染色体;rs12779637)、2-羟基异戊酰肉碱(21号染色体;rs1571700)、硬脂酰肉碱(1号染色体;rs3811444)和天冬氨酸性状(8号染色体;rs750472)血液水平相关的新位点。基于对血液单核细胞中表达数量性状位点的综合分析以及基因表达与代谢物水平之间的相关性,我们为推定的致病基因提供了证据:总酰基肉碱的SLC22A16、精氨酸的ARG1、2-羟基异戊酰肉碱的HLCS、通过1号染色体上的反式效应作用于硬脂酰肉碱的JAM3以及天冬氨酸性状的PPP1R16A。此外,我们报告了先前在血浆、血清或尿液中测量的代谢物的10个位点的重复验证,并提供了额外的功能证据。总之,我们对单核苷酸多态性(SNP)、基因表达和代谢物数据的综合分析指出了可能参与人类代谢调节的新遗传因素。在几个位点,我们通过基因表达为代谢物调节提供了证据,并观察到与常见疾病的全基因组关联研究位点存在重叠。这些结果为后续的功能和疾病相关研究提供了有力的理论依据。