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智利枫糖尿症(MSUD)患儿的能量消耗

Energy Expenditure in Chilean Children with Maple Syrup Urine Disease (MSUD).

作者信息

Campo Karen, Castro Gabriela, Hamilton Valerie, Cabello Juan Francisco, Raimann Erna, Arias Carolina, Cornejo Verónica

机构信息

INTA - Instituto de Nutrición y TecnologÚa de Alimentos Doctor Fernando Monckeberg Barro, University of Chile, Av. El Líbano 5524, Macul, Macul, Santiago, Chile.

出版信息

JIMD Rep. 2016;26:69-76. doi: 10.1007/8904_2015_500. Epub 2015 Oct 13.

Abstract

INTRODUCTION

Maple syrup urine disease (MSUD) is an autosomal recessive disorder caused by a blockage of branched-chain keto acid of BCAA (branched-chain keto acid dehydrogenase, BCKDH) leading to neurological damage induced by accumulation of leucine and metabolites. MSUD expenditure and energy requirement information is limited.

OBJECTIVE

To determine if basal/total energy expenditure (BEE/TEE) is comparable between different determination methods and if values agree with recommendations of energy in MSUD children, and whether they relate to nutritional status.

METHODS

Case-control study between MSUD (n = 16) and healthy children (n = 11) aged 6-18 years. Current nutritional status, physical activity level, body composition by DEXA and BEE/TEE by indirect calorimetry (BEEr) and predictive equations (FAO/WHO/ONU - WHO - and Schofield) were assessed; STATA 2013 (p < 0.05).

RESULTS

When comparing the energy expenditure variables, there was no significant difference between groups. Moreover, compared to BEEr, equations underestimate according to BEE WHO and Schofield, respectively (P = 0.00; 0.02). The WHO equation had lower average calorie difference, greater concordance correlation and association with indirect calorimetry compared to the Schofield equation for both groups, being the best predictor of the BEE for MSUD group.

CONCLUSION

Energy recommendations for MSUD children are according to energy expenditure; thus the use of WHO equation is a clinically and statistically feasible tool for its determination.

摘要

引言

枫糖尿症(MSUD)是一种常染色体隐性疾病,由支链氨基酸(BCAA)的支链酮酸(支链酮酸脱氢酶,BCKDH)受阻引起,导致亮氨酸及其代谢产物积累引发神经损伤。关于MSUD的能量消耗和能量需求信息有限。

目的

确定不同测定方法之间基础/总能量消耗(BEE/TEE)是否具有可比性,以及这些值是否符合MSUD患儿的能量推荐标准,它们是否与营养状况相关。

方法

对16例6至18岁的MSUD患儿和11例健康儿童进行病例对照研究。评估当前营养状况、身体活动水平、通过双能X线吸收法(DEXA)测定的身体成分以及通过间接测热法(BEEr)和预测方程(粮农组织/世界卫生组织/联合国 - 世界卫生组织 - 和斯科菲尔德方程)测定的BEE/TEE;使用STATA 2013软件(p < 0.05)。

结果

比较能量消耗变量时,各组之间无显著差异。此外,与BEEr相比,WHO和斯科菲尔德方程分别低估了BEE(P = 0.00;0.02)。对于两组而言,WHO方程的平均卡路里差异更低,一致性相关性更高,与间接测热法的关联性更强,是MSUD组BEE的最佳预测指标。

结论

MSUD患儿的能量推荐应依据能量消耗;因此,使用WHO方程是一种在临床和统计学上可行的测定工具。

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