Villegas Ana, Arrizabalaga Beatriz, Bonanad Santiago, Colado Enrique, Gaya Anna, González Ataúlfo, Jarque Isidro, Núñez Ramiro, Ojeda Emilio, Orfao Alberto, Ribera José-María, Vicente Vicente, Urbano-Ispizua Álvaro
Servicio de Hematología, Hospital Clínico San Carlos de Madrid, Madrid, España.
Servicio de Hematología, Hospital Cruces, Bilbao, España.
Med Clin (Barc). 2016 Mar 18;146(6):278.e1-7. doi: 10.1016/j.medcli.2015.12.012. Epub 2016 Feb 17.
Paroxysmal nocturnal haemoglobinuria (PNH) is an acquired clonal disorder of the haematopoietic progenitor cells due to a somatic mutation in theX-linked phosphatidylinositol glycan class A gene. The disease is characterized by intravascular haemolytic anaemia, propensity to thromboembolic events and bone marrow failure. Other direct complications of haemolysis include dysphagia, erectile dysfunction, abdominal pain, asthenia and chronic renal failure (65% of patients). The disease appears more often in the third decade of life and there is no sex or age preference. Detection of markers associated with glucosyl phosphatidyl inositol deficit by flow cytometry is currently used in the diagnosis of PNH. For years, transfusions have been the mainstay of therapy for PNH. A breakthrough in treatment has been the approval of the humanized monoclonal antibody eculizumab, which works by blocking the C5 complement protein, preventing its activation and therefore haemolysis. Several studies have confirmed that treatment with eculizumab avoids or decreases the need for transfusions, decreases the probability of thrombosis, improves the associated symptomatology and the quality of life in patients with PNH, showing an increase in survival. Because of rapid advances in the knowledge of the disease and its treatment, it may become necessary to adapt and standardize clinical guidelines for the management of patients with PNH.
阵发性睡眠性血红蛋白尿(PNH)是一种获得性造血祖细胞克隆性疾病,由X连锁磷脂酰肌醇聚糖A类基因的体细胞突变引起。该疾病的特征为血管内溶血、易发生血栓栓塞事件和骨髓衰竭。溶血的其他直接并发症包括吞咽困难、勃起功能障碍、腹痛、乏力和慢性肾衰竭(65%的患者)。该疾病多在生命的第三个十年出现,无性别或年龄偏好。目前通过流式细胞术检测与糖基磷脂酰肌醇缺乏相关的标志物用于PNH的诊断。多年来,输血一直是PNH治疗的主要手段。治疗上的一个突破是批准了人源化单克隆抗体依库珠单抗,其作用机制是阻断C5补体蛋白,防止其激活从而避免溶血。多项研究证实,依库珠单抗治疗可避免或减少输血需求,降低血栓形成的可能性,改善PNH患者的相关症状和生活质量,显示出生存率提高。由于对该疾病及其治疗的认识迅速发展,可能有必要调整和规范PNH患者管理的临床指南。