伴有嗜酸性粒细胞增多的血管淋巴样增生及尺神经受压
Angiolymphoid hyperplasia with eosinophilia and entrapment of the ulnar nerve.
作者信息
Di Vitantonio Hambra, De Paulis Danilo, Ricci Alessandro, Raysi Soheila Dehcordi, Marzi Sara, Del Maestro Mattia, Galzio Renato Juan
机构信息
Department of Life, Health and Environmental Sciences (MESVA), University of L'Aquila, L'Aquila, Italy.
Department of Neurosurgery, San Salvatore city Hospital, L'Aquila, Italy.
出版信息
Surg Neurol Int. 2016 Mar 2;7(Suppl 5):S160-3. doi: 10.4103/2152-7806.177896. eCollection 2016.
BACKGROUND
The angiolymphoid hyperplasia with eosinophilia (ALHE) is a sporadic vasoproliferative lesion of uncertain etiology involving the skin and the subcutaneous tissue. Occasionally, it involves also the large arteries compressing the near nerves. ALHE is commonly confused with Kimura's disease because of their clinical and histological similarities.
CASE DESCRIPTION
We report a case of a 52-year-old female suffering from a 6-month pain and paresthesias in the fourth and fifth finger of the right hand. The angiography showed a pseudoaneurysm in the proximal third of the right ulnar artery. A complete surgical excision of the vascular lesion was undertaken. The lesion forced the right ulnar nerve. The histopathological diagnosis deposed for ALHE.
CONCLUSION
Up to now, literature has described 8 cases of ALHE involving the arteries, and only one case originating from the ulnar nerve. The authors report a case of a female with ALHE involving the ulnar artery that compressed the ulnar nerve. Clinical aspects, radiological features, surgical treatment, and operative findings are discussed reviewing the pertinent literature.
背景
嗜酸性粒细胞增多性血管淋巴样增生（ALHE）是一种病因不明的散发性血管增生性病变，累及皮肤和皮下组织。偶尔，它也会累及压迫附近神经的大动脉。由于其临床和组织学相似性，ALHE常与木村病混淆。
病例描述
我们报告一例52岁女性，右手第四和第五指疼痛和感觉异常6个月。血管造影显示右尺动脉近端三分之一处有一个假性动脉瘤。对血管病变进行了完整的手术切除。病变压迫右尺神经。组织病理学诊断为ALHE。
结论
迄今为止，文献报道了8例累及动脉的ALHE，仅有1例起源于尺神经。作者报告了一例女性ALHE累及尺动脉并压迫尺神经的病例。结合相关文献讨论了临床特征、影像学表现、手术治疗及手术所见。
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