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亨廷顿基因对正常神经发育的性别特异性影响。

Sex-specific effects of the Huntington gene on normal neurodevelopment.

作者信息

Lee Jessica K, Ding Yue, Conrad Amy L, Cattaneo Elena, Epping Eric, Mathews Kathy, Gonzalez-Alegre Pedro, Cahill Larry, Magnotta Vincent, Schlaggar Bradley L, Perlmutter Joel S, Kim Regina E Y, Dawson Jeffrey D, Nopoulos Peg

机构信息

Department of Psychiatry, University of Iowa Carver College of Medicine, Iowa City, Iowa.

Department of Pediatrics, University of Iowa Carver College of Medicine, Iowa City, Iowa.

出版信息

J Neurosci Res. 2017 Jan 2;95(1-2):398-408. doi: 10.1002/jnr.23980.

DOI:10.1002/jnr.23980
PMID:27870408
原文链接:https://pmc.ncbi.nlm.nih.gov/articles/PMC5729280/
Abstract

Huntington disease is a neurodegenerative disorder caused by a gene (HTT) with a unique feature of trinucleotide repeats ranging from 10 to 35 in healthy people; when expanded beyond 39 repeats, Huntington disease develops. Animal models demonstrate that HTT is vital to brain development; however, this has not been studied in humans. Moreover, evidence suggests that triplet repeat genes may have been vital in evolution of the human brain. Here we evaluate brain structure using magnetic resonance imaging and brain function using cognitive tests in a sample of school-aged children ages 6 to 18 years old. DNA samples were processed to quantify the number of CAG repeats within HTT. We find that the number of repeats in HTT, below disease threshold, confers advantageous changes in brain structure and general intelligence (IQ): the higher the number of repeats, the greater the change in brain structure, and the higher the IQ. The pattern of structural brain changes associated with HTT is strikingly different between males and females. HTT may confer an advantage or a disadvantage depending on the repeat length, playing a key role in either the evolution of a superior human brain or development of a uniquely human brain disease. © 2016 Wiley Periodicals, Inc.

摘要

亨廷顿舞蹈症是一种神经退行性疾病,由一个基因(HTT)引起,该基因具有独特的三核苷酸重复序列特征,在健康人群中其重复次数为10至35次;当重复次数超过39次时,就会引发亨廷顿舞蹈症。动物模型表明HTT对大脑发育至关重要;然而,这一点尚未在人类身上得到研究。此外,有证据表明三联体重复基因可能在人类大脑的进化过程中发挥了重要作用。在此,我们对6至18岁学龄儿童样本进行了磁共振成像脑结构评估和认知测试脑功能评估。对DNA样本进行处理,以量化HTT内CAG重复序列的数量。我们发现,在疾病阈值以下,HTT中的重复次数会给脑结构和一般智力(智商)带来有利变化:重复次数越高,脑结构变化越大,智商越高。与HTT相关的脑结构变化模式在男性和女性之间存在显著差异。根据重复长度的不同,HTT可能带来优势或劣势,在人类优越大脑的进化或独特的人类脑部疾病的发展中发挥关键作用。© 2016威利期刊公司

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本文引用的文献

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Sex Influences on the Brain: An Issue Whose Time Has Come.性别对大脑的影响:是时候正视这个问题了。
Neuron. 2015 Dec 16;88(6):1084-1085. doi: 10.1016/j.neuron.2015.11.021.
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Abnormal cerebellar volume and corticocerebellar dysfunction in early manifest Huntington's disease.早期亨廷顿舞蹈病患者小脑体积异常和皮质小脑功能障碍。
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Mutant Huntingtin Drives Development of an Advantageous Brain Early in Life: Evidence in Support of Antagonistic Pleiotropy.突变亨廷顿蛋白驱动生命早期大脑的有利发育:拮抗多效性的证据。
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