Schrettl Verena, Felgenhauer Norbert, Rabe Christian, Fernando Malkanthi, Eyer Florian
a Department of Clinical Toxicology , Klinikum Rechts der Isar, Technical University of Munich (TUM) , Munich , Germany.
b Laboratory of Clinical Biochemistry and Metabolism , Center for Pediatrics and Adolescent Medicine Freiburg, University Freiburg , Freiburg , Germany.
Clin Toxicol (Phila). 2017 Apr;55(4):260-266. doi: 10.1080/15563650.2017.1284333. Epub 2017 Feb 3.
Valproic acid and its metabolites - particularly valproyl-CoA - are inhibitors of the enzyme N-acetylglutamate synthetase. The amino acid l-arginine can stimulate N-acetylglutamate synthetase activity and could be potentially used therapeutically to correct hyperammonemia caused by valproate therapy or overdose. Severely valproic-acid-poisoned patients are usually treated with l-carnitine or hemodialysis in order to decrease hyperammonemia. We herein report of five cases, in which l-arginine was administered.
Observational study on five cases. Patients with hyperammonemia (i.e., ammonia 80 > μg/dL) and symptoms consistent with valproate overdose (i.e., drowsiness, coma) were selected for treatment with l-arginine. Data was collected retrospectively.
l-Arginine decreased ammonia levels in a close temporal relation (case I ammonia in EDTA-plasma [μg/dL] decreased from 381 to 39; case II from 281 to 50; case III from 669 to 74; case IV from 447 to 56; case V from 202 to 60). In cases I and II, hemodialysis was performed and l-carnitine was given before the administration of l-arginine. In case III, hemodialysis was performed after the administration of l-arginine was already started. In cases IV and V, treatment with l-arginine was the sole measure to decrease ammonia levels in plasma.
The results suggest that l-arginine may be beneficial in selected cases of valproate overdose complicated by hyperammonemia. l-Arginine could extend our conventional treatment options for valproic acid overdose.
丙戊酸及其代谢产物——尤其是丙戊酰辅酶A——是N - 乙酰谷氨酸合成酶的抑制剂。氨基酸L - 精氨酸可刺激N - 乙酰谷氨酸合成酶的活性,有可能用于治疗因丙戊酸盐治疗或过量用药引起的高氨血症。重度丙戊酸中毒患者通常接受L - 肉碱治疗或血液透析以降低高氨血症。我们在此报告5例使用L - 精氨酸治疗的病例。
对5例病例进行观察性研究。选择有高氨血症(即氨水平>80μg/dL)且有与丙戊酸盐过量相符症状(即嗜睡、昏迷)的患者接受L - 精氨酸治疗。数据进行回顾性收集。
L - 精氨酸在短时间内降低了氨水平(病例I:乙二胺四乙酸血浆中的氨[μg/dL]从381降至39;病例II从281降至50;病例III从669降至74;病例IV从447降至56;病例V从202降至60)。在病例I和II中,在给予L - 精氨酸之前进行了血液透析并给予了L - 肉碱。在病例III中,在已经开始给予L - 精氨酸后进行了血液透析。在病例IV和V中,使用L - 精氨酸治疗是降低血浆氨水平的唯一措施。
结果表明,L - 精氨酸可能对某些合并高氨血症的丙戊酸盐过量病例有益。L - 精氨酸可为我们治疗丙戊酸过量提供更多的常规治疗选择。