• 文献检索
  • 文档翻译
  • 深度研究
  • 学术资讯
  • Suppr Zotero 插件Zotero 插件
  • 邀请有礼
  • 套餐&价格
  • 历史记录
应用&插件
Suppr Zotero 插件Zotero 插件浏览器插件Mac 客户端Windows 客户端微信小程序
定价
高级版会员购买积分包购买API积分包
服务
文献检索文档翻译深度研究API 文档MCP 服务
关于我们
关于 Suppr公司介绍联系我们用户协议隐私条款
关注我们

Suppr 超能文献

核心技术专利:CN118964589B侵权必究
粤ICP备2023148730 号-1Suppr @ 2026

文献检索

告别复杂PubMed语法,用中文像聊天一样搜索,搜遍4000万医学文献。AI智能推荐,让科研检索更轻松。

立即免费搜索

文件翻译

保留排版,准确专业,支持PDF/Word/PPT等文件格式,支持 12+语言互译。

免费翻译文档

深度研究

AI帮你快速写综述,25分钟生成高质量综述,智能提取关键信息,辅助科研写作。

立即免费体验

血管性埃勒斯-当洛综合征的诊断、自然病史及管理

Diagnosis, natural history, and management in vascular Ehlers-Danlos syndrome.

作者信息

Byers Peter H, Belmont John, Black James, De Backer Julie, Frank Michael, Jeunemaitre Xavier, Johnson Diana, Pepin Melanie, Robert Leema, Sanders Lynn, Wheeldon Nigel

出版信息

Am J Med Genet C Semin Med Genet. 2017 Mar;175(1):40-47. doi: 10.1002/ajmg.c.31553.

DOI:10.1002/ajmg.c.31553
PMID:28306228
Abstract

Vascular Ehlers Danlos syndrome (vEDS) is an uncommon genetic disorders characterized by arterial aneurysm, dissection and rupture, bowel rupture, and rupture of the gravid uterus. The frequency is estimated as 1/50,000-1/200,000 and results from pathogenic variants in COL3A1, which encodes the chains of type III procollagen, a major protein in vessel walls and hollow organs. Initial diagnosis depends on the recognitions of clinical features, including family history. Management is complex and requires multiple specialists who can respond to and manage the major complications. A summary of recommendations for management include: Identify causative variants in COL3A1 prior to application of diagnosis, modulate life style to minimize injury, risk of vessel/organ rupture, identify and create care team, provide individual plans for emergency care ("vascular EDS passport") with diagnosis and management plan for use when traveling, centralize management at centers of excellence (experience) when feasible, maintain blood pressure in the normal range and treat hypertension aggressively, surveillance of vascular tree by doppler ultrasound, CTA (low radiation alternatives) or MRA if feasible on an annual basis. These recommendations represent a consensus of an international group of specialists with a broad aggregate experience in the care of individuals with vascular EDS that will need to be assessed on a regular basis as new information develops. © 2017 Wiley Periodicals, Inc.

摘要

血管型埃勒斯-当洛综合征(vEDS)是一种罕见的遗传性疾病,其特征为动脉动脉瘤、夹层和破裂、肠道破裂以及妊娠子宫破裂。估计发病率为1/50,000 - 1/200,000,由COL3A1基因的致病性变异引起,该基因编码III型前胶原链,这是血管壁和中空器官中的一种主要蛋白质。初始诊断取决于对临床特征的识别,包括家族史。管理复杂,需要多个专科医生来应对和处理主要并发症。管理建议总结如下:在进行诊断之前确定COL3A1中的致病变异,调整生活方式以尽量减少损伤、血管/器官破裂的风险,确定并组建护理团队,提供针对紧急护理的个人计划(“血管EDS护照”),包括诊断和管理计划以便在旅行时使用,在可行的情况下由卓越中心(有经验的)进行集中管理,将血压维持在正常范围并积极治疗高血压,每年可行时通过多普勒超声、CTA(低辐射替代方法)或MRA对血管系统进行监测。这些建议代表了一组在血管EDS患者护理方面具有广泛综合经验的国际专家的共识,随着新信息的出现,需要定期对其进行评估。© 2017威利期刊公司

相似文献

1
Diagnosis, natural history, and management in vascular Ehlers-Danlos syndrome.血管性埃勒斯-当洛综合征的诊断、自然病史及管理
Am J Med Genet C Semin Med Genet. 2017 Mar;175(1):40-47. doi: 10.1002/ajmg.c.31553.
2
Vascular Ehlers-Danlos Syndrome血管性埃勒斯-当洛综合征
3
A multi-institutional experience in the aortic and arterial pathology in individuals with genetically confirmed vascular Ehlers-Danlos syndrome.遗传性血管型埃勒斯-当洛斯综合征患者的主动脉和动脉病理学的多机构经验。
J Vasc Surg. 2019 Nov;70(5):1543-1554. doi: 10.1016/j.jvs.2019.01.069. Epub 2019 May 21.
4
A multi-institutional experience in vascular Ehlers-Danlos syndrome diagnosis.血管型埃勒斯-当洛斯综合征的多机构诊断经验。
J Vasc Surg. 2020 Jan;71(1):149-157. doi: 10.1016/j.jvs.2019.04.487. Epub 2019 Jul 26.
5
Splenic artery pathology presentation, operative interventions, and outcomes in 88 patients with vascular Ehlers-Danlos syndrome.88 例血管型埃勒斯-当洛斯综合征患者的脾动脉病变表现、手术干预及结果。
J Vasc Surg. 2023 Aug;78(2):394-404. doi: 10.1016/j.jvs.2023.04.007. Epub 2023 Apr 15.
6
A Novel Frameshift COL3A1 Variant in Vascular Ehlers-Danlos Syndrome.血管性埃勒斯-当洛综合征中的一种新型移码COL3A1变异体。
Ann Vasc Surg. 2019 Nov;61:472.e9-472.e13. doi: 10.1016/j.avsg.2019.05.057. Epub 2019 Aug 5.
7
Vascular Ehlers-Danlos Syndrome With a Novel Missense COL3A1 Mutation Present With Pulmonary Complications and Iliac Arterial Dissection.伴有新型错义COL3A1突变的血管型埃勒斯-当洛综合征出现肺部并发症和髂动脉夹层。
Vasc Endovascular Surg. 2018 Feb;52(2):138-142. doi: 10.1177/1538574417745432. Epub 2017 Dec 7.
8
Vascular Ehlers-Danlos syndrome.血管型埃勒斯-当洛综合征
Ann Genet. 2004 Jan-Mar;47(1):1-9. doi: 10.1016/j.anngen.2003.07.002.
9
Six uneventful pregnancy outcomes in an extended vascular Ehlers-Danlos syndrome family.一个患有扩展性血管型埃勒斯-当洛综合征的家族中有六例顺利的妊娠结局。
Am J Med Genet A. 2017 Feb;173(2):519-523. doi: 10.1002/ajmg.a.38033. Epub 2016 Nov 7.
10
Vascular Ehlers-Danlos syndrome: pathophysiology, diagnosis, and prevention and treatment of its complications.血管型埃勒斯-当洛斯综合征:病理生理学、诊断以及并发症的预防和治疗。
Cardiol Rev. 2012 Jan-Feb;20(1):4-7. doi: 10.1097/CRD.0b013e3182342316.

引用本文的文献

1
Case Report: A rare presentation of vascular Ehlers-Danlos syndrome with a massive hemothorax and a chest wall hematoma.病例报告:血管型埃勒斯-当洛综合征的罕见表现,伴有大量血胸和胸壁血肿。
Front Med (Lausanne). 2025 Aug 8;12:1648439. doi: 10.3389/fmed.2025.1648439. eCollection 2025.
2
Diagnosis of vascular Ehlers Danlos syndrome and management of vascular complications: a vascular surgeons perspective.血管性埃勒斯-当洛综合征的诊断及血管并发症的处理:血管外科医生的观点
Med Genet. 2024 Dec 3;36(4):255-259. doi: 10.1515/medgen-2024-2053. eCollection 2024 Dec.
3
Early diagnosis of vascular Ehlers-Danlos syndrome through AI-powered facial analysis: Results from the Montalcino Aortic Consortium.
通过人工智能面部分析早期诊断血管性埃勒斯-当洛综合征:蒙塔尔奇诺主动脉联盟的结果。
Genet Med Open. 2025 May 9;3:103434. doi: 10.1016/j.gimo.2025.103434. eCollection 2025.
4
The Incidence of Misdiagnosis in Patients with Ehlers-Danlos Syndrome.埃勒斯-当洛综合征患者的误诊发生率
Children (Basel). 2025 May 29;12(6):698. doi: 10.3390/children12060698.
5
Prevalence of vascular complications in Ehlers-Danlos syndrome: a systematic review and meta-analysis.埃勒斯-当洛综合征血管并发症的患病率:一项系统评价和荟萃分析。
Orphanet J Rare Dis. 2025 Jun 20;20(1):312. doi: 10.1186/s13023-025-03854-6.
6
Arteriovenous fistula following radial artery cannulation in a patient with vascular Ehlers-Danlos syndrome.一名患有血管性埃勒斯-当洛综合征的患者在桡动脉置管后发生动静脉瘘。
J Vasc Surg Cases Innov Tech. 2025 Apr 28;11(4):101822. doi: 10.1016/j.jvscit.2025.101822. eCollection 2025 Aug.
7
Hematomas after coughing: a case description of vascular Ehlers-Danlos syndrome.咳嗽后出现血肿:血管性埃勒斯-当洛综合征病例描述
Quant Imaging Med Surg. 2025 May 1;15(5):4864-4867. doi: 10.21037/qims-24-2080. Epub 2025 Apr 28.
8
Management of Direct Internal Carotid-Cavernous Sinus Fistula in a Patient with Ehlers-Danlos Syndrome: A Case Study on Selective Transvenous Embolization Using Coils and -Butyl-2-Cyanoacrylate.一名患有埃勒斯-当洛综合征患者的颈内动脉-海绵窦直接瘘的管理:关于使用线圈和丁基-2-氰基丙烯酸酯进行选择性经静脉栓塞的病例研究
J Neuroendovasc Ther. 2025;19(1). doi: 10.5797/jnet.cr.2024-0121. Epub 2025 May 8.
9
The chemical chaperone 4-phenylbutyric acid rescues molecular cell defects of COL3A1 mutations that cause vascular Ehlers Danlos Syndrome.化学伴侣4-苯基丁酸可挽救导致血管性埃勒斯-当洛综合征的COL3A1突变的分子细胞缺陷。
Cell Death Discov. 2025 Apr 25;11(1):200. doi: 10.1038/s41420-025-02476-y.
10
Identification and Structural Characterization of a Novel COL3A1 Gene Duplication in a Family With Vascular Ehlers-Danlos Syndrome.血管性埃勒斯-当洛综合征家系中一个新的COL3A1基因重复的鉴定与结构特征分析
Mol Genet Genomic Med. 2025 Apr;13(4):e70095. doi: 10.1002/mgg3.70095.