Bowers Daniel C, Moskowitz Chaya S, Chou Joanne F, Mazewski Claire M, Neglia Joseph P, Armstrong Gregory T, Leisenring Wendy M, Robison Leslie L, Oeffinger Kevin C
Daniel C. Bowers, UT Southwestern Medical Center, Dallas, TX; Chaya S. Moskowitz, Joanne F. Chou, and Kevin C. Oeffinger, Memorial Sloan Kettering Cancer Center, New York, NY; Claire M. Mazewski, Emory University, Atlanta, GA; Joseph P. Neglia, University of Minnesota, Minneapolis, MN; Gregory T. Armstrong and Leslie L. Robison, St. Jude Children's Research Hospital, Memphis, TN; and Wendy M. Leisenring, Fred Hutchinson Cancer Research Center, Seattle, WA.
J Clin Oncol. 2017 May 10;35(14):1570-1576. doi: 10.1200/JCO.2016.70.1896. Epub 2017 Mar 24.
Purpose Little is known about neurologic morbidity attributable to cranial radiotherapy (CRT) -associated meningiomas. Materials and Methods From 4,221 survivors exposed to CRT in the Childhood Cancer Survivor Study, a diagnosis of meningioma and onset of neurologic sequelae were ascertained. Cox proportional hazards regression was used to estimate hazard ratios (HR) and 95% CIs to evaluate the factors associated with neurologic sequelae after subsequent meningioma. Results One hundred ninety-nine meningiomas were identified among 169 participants. The median interval from primary cancer to meningioma diagnosis was 22 years (5 to 37 years). The cumulative incidence of a subsequent meningioma by age 40 years was 5.6% (95% CI, 4.7% to 6.7%). CRT doses of 20 to 29.9 Gy (HR, 1.6; 95% CI,1.0 to 2.6) and doses ≥ 30 Gy (HR, 2.6; 95% CI, 1.6 to 4.2) were associated with an increased risk of meningioma compared with CRT doses of 1.5 to 19.9 Gy ( P < .001). Within 6 months before or subsequent to a meningioma diagnosis, 20% (30 of 149) reported at least one new neurologic sequela, including seizures (8.3%), auditory-vestibular-visual deficits (6%), focal neurologic dysfunction (7.1%), and severe headaches (5.3%). Survivors reporting a meningioma had increased risks of neurologic sequelae > 5 years after primary cancer diagnosis, including seizures (HR, 10.0; 95% CI, 7.0 to 15.3); auditory-vestibular-visual sensory deficits (HR, 2.3; 95% CI, 1.3 to 4.0); focal neurologic dysfunction (HR, 4.9; 95% CI, 3.2 to 7.5); and severe headaches (HR, 3.2; 95% CI, 1.9 to 5.4). With a median follow-up of 72 months after meningioma diagnosis (range, 3.8 to 395 months), 22 participants (13%) were deceased, including six deaths attributed to a meningioma. Conclusion Childhood cancer survivors exposed to CRT and subsequently diagnosed with a meningioma experience significant neurologic morbidity.
目的 关于颅部放射治疗(CRT)相关脑膜瘤所致神经疾病的发病率,人们了解甚少。材料与方法 在儿童癌症幸存者研究中,对4221名接受过CRT的幸存者进行了调查,确定了脑膜瘤的诊断情况和神经后遗症的发病情况。采用Cox比例风险回归模型来估计风险比(HR)和95%置信区间(CI),以评估后续发生脑膜瘤后与神经后遗症相关的因素。结果 在169名参与者中识别出199例脑膜瘤。从原发性癌症到脑膜瘤诊断的中位间隔时间为22年(5至37年)。到40岁时后续发生脑膜瘤的累积发病率为5.6%(95%CI,4.7%至6.7%)。与1.5至19.9 Gy的CRT剂量相比,20至29.9 Gy的CRT剂量(HR,1.6;95%CI,1.0至2.6)和≥30 Gy的剂量(HR,2.6;95%CI,1.6至4.2)与脑膜瘤风险增加相关(P <.001)。在脑膜瘤诊断前6个月内或之后,20%(149例中的30例)报告至少出现一种新的神经后遗症,包括癫痫发作(8.3%)、听觉 - 前庭 - 视觉缺陷(6%)、局灶性神经功能障碍(7.1%)和严重头痛(5.3%)。报告患有脑膜瘤的幸存者在原发性癌症诊断后>5年出现神经后遗症的风险增加,包括癫痫发作(HR,10.0;95%CI,7.0至15.3);听觉 - 前庭 - 视觉感觉缺陷(HR,2.3;95%CI,1.3至4.0);局灶性神经功能障碍(HR,4.9;95%CI,3.2至7.5);以及严重头痛(HR,3.2;95%CI,1.9至5.4)。在脑膜瘤诊断后中位随访72个月(范围,3.8至395个月)时,22名参与者(13%)死亡,其中6例死亡归因于脑膜瘤。结论 接受CRT并随后被诊断为脑膜瘤的儿童癌症幸存者经历了显著的神经疾病发病率。