Hanusova Zdenka, Mosko Tibor, Matej Radoslav, Holada Karel
Institute of Immunology and Microbiology, First Faculty of Medicine, Charles University, Studnickova 7, Prague 2, 128 00, Czech Republic.
Department of Pathology and Molecular Medicine, Thomayer Teaching Hospital, Videnska 800, Prague 4, 14059, Czech Republic.
J Gen Virol. 2017 Jun;98(6):1563-1569. doi: 10.1099/jgv.0.000803. Epub 2017 Jun 14.
Proteinase-activated receptor 2 (PAR2) is suspected to modulate the pathogenesis of various neurodegenerative conditions. We previously described delayed onset of clinical symptoms and prolonged survival of PAR2-deficient mice after intracerebral inoculation with prions. Here we report the results from a refined blinded study that aimed to investigate the effects of PAR2 deletion on scrapie pathogenesis after peripheral infection. This study failed to confirm that PAR2 deficiency impacts on the length of the incubation period, with PAR2-/- and PAR2+/+ littermates developing scrapie at the same time. To clarify the discrepancy between the two observations, we repeated the intracerebral inoculation study while utilizing our refined protocol, which aimed to limit possible sources of experimental bias. The study again failed to confirm the significant effect of PAR2 expression on the course of prion infection. Our report emphasizes and discusses the importance of unbiased experimental design and the selection of proper genetic controls when using genetically altered animal models for prion pathogenesis studies.
蛋白酶激活受体2(PAR2)被怀疑参与多种神经退行性疾病的发病机制调节。我们之前曾描述过,在用朊病毒进行脑内接种后,PAR2基因缺陷小鼠的临床症状出现延迟且存活时间延长。在此,我们报告一项精确的双盲研究结果,该研究旨在探讨PAR2基因缺失对外周感染后羊瘙痒病发病机制的影响。这项研究未能证实PAR2基因缺陷会影响潜伏期的长短,PAR2基因敲除小鼠(PAR2-/-)和野生型同窝小鼠(PAR2+/+)同时出现羊瘙痒病症状。为了阐明这两项观察结果之间的差异,我们采用改进后的方案重复了脑内接种研究,旨在减少可能的实验偏差来源。该研究再次未能证实PAR2表达对朊病毒感染进程有显著影响。我们的报告强调并讨论了在使用基因改造动物模型进行朊病毒发病机制研究时,无偏倚实验设计和选择合适遗传对照的重要性。