Park Jae Woo, Kim Chul-Hwan, Moon Chan Woong
Department of Oral and Maxillofacial Surgery, College of Dentistry, Dankook University, Cheonan, Korea.
J Korean Assoc Oral Maxillofac Surg. 2017 Aug;43(4):262-266. doi: 10.5125/jkaoms.2017.43.4.262. Epub 2017 Aug 24.
Hemangioma is the most common benign tumor of a vascular origin, and is characterized by the abnormal proliferation of blood vessels. Intramuscular hemangioma (IMH) usually involves the skeletal muscles of the trunk or limbs, but rarely occurs in the head and neck region. This case report presents a patient with IMH showing multiple phleboliths in the buccal cheek. A 13-year-old boy was referred for the evaluation and management of painful swelling of the left cheek that had gradually increased in size over a 6 year duration. The examination revealed a palpable firm mass. Reddish-blue buccal mucosa color was observed with an aciniform shape. Preoperative magnetic resonance imaging (MRI) showed a vascular tumor in the left side adjacent to the buccinator and depressor orbicularis oris muscles. Surgical resection under general anesthesia was performed via the intraoral approach. The mass and phleboliths were extracted successfully. A histopathological examination confirmed the diagnosis of IMH. In conclusion, clinicians should be aware of the possibility of IMH in cases of a palpable mass with multiple nodules deep within the muscle in the buccal cheek. Among the several diagnostic tools, MRI provides essential information on the extent and surrounding anatomy of IMH.
血管瘤是最常见的血管源性良性肿瘤,其特征为血管异常增殖。肌内血管瘤(IMH)通常累及躯干或四肢的骨骼肌,但很少发生于头颈部区域。本病例报告介绍了一名患有IMH的患者,其颊部出现多个静脉石。一名13岁男孩因左侧颊部疼痛性肿胀前来就诊,该肿胀在6年时间里逐渐增大。检查发现可触及一个质地坚硬的肿块。观察到颊黏膜呈红蓝色,呈腺泡状。术前磁共振成像(MRI)显示左侧靠近颊肌和口轮匝肌下压肌处有一个血管性肿瘤。在全身麻醉下通过口腔内入路进行手术切除。成功摘除了肿块和静脉石。组织病理学检查确诊为IMH。总之,对于颊部肌肉深处可触及有多个结节的肿块病例,临床医生应意识到存在IMH的可能性。在几种诊断工具中,MRI提供了有关IMH范围及周围解剖结构的重要信息。