Department of Neurosurgery, Boston Children's Hospital, Harvard Medical School, Boston, MA, United States; Department of Neurology, Boston Children's Hospital, Harvard Medical School, Boston, MA, United States; F.M. Kirby Center for Neurobiology, Boston Children's Hospital, Harvard Medical School, Boston, MA, United States.
Department of Neurosurgery, Boston Children's Hospital, Harvard Medical School, Boston, MA, United States.
Exp Neurol. 2018 Apr;302:1-13. doi: 10.1016/j.expneurol.2017.12.010. Epub 2017 Dec 26.
Children who are born preterm are at risk for encephalopathy of prematurity, a leading cause of cerebral palsy, cognitive delay and behavioral disorders. Current interventions are limited and none have been shown to reverse cognitive and behavioral impairments, a primary determinant of poor quality of life for these children. Moreover, the mechanisms of perinatal brain injury that result in functional deficits and imaging abnormalities in the mature brain are poorly defined, limiting the potential to target interventions to those who may benefit most. To determine whether impairments are reversible after a prenatal insult, we investigated a spectrum of functional deficits and diffusion tensor imaging (DTI) abnormalities in young adult animals. We hypothesized that prenatal transient systemic hypoxia-ischemia (TSHI) would induce multiple functional deficits concomitant with reduced microstructural white and gray matter integrity, and tested whether these abnormalities could be ameliorated using postnatal erythropoietin (EPO), an emerging neurorestorative intervention. On embryonic day 18 uterine arteries were transiently occluded for 60min via laparotomy. Shams underwent anesthesia and laparotomy for 60min. Pups were born and TSHI pups were randomized to receive EPO or vehicle via intraperitoneal injection on postnatal days 1 to 5. Gait, social interaction, olfaction and open field testing was performed from postnatal day 25-35 before brains underwent ex vivo DTI to measure fractional anisotropy, axial diffusivity and radial diffusivity. Prenatal TSHI injury causes hyperactivity, impaired gait and poor social interaction in young adult rats that mimic the spectrum of deficits observed in children born preterm. Collectively, these data show for the first time in a model of encephalopathy of prematurity that postnatal EPO treatment mitigates impairments in social interaction, in addition to gait deficits. EPO also normalizes TSHI-induced microstructural abnormalities in fractional anisotropy and radial diffusivity in multiple regions, consistent with improved structural integrity and recovery of myelination. Taken together, these results show behavioral and memory deficits from perinatal brain injury are reversible. Furthermore, resolution of DTI abnormalities may predict responsiveness to emerging interventions, and serve as a biomarker of CNS injury and recovery.
早产儿易患早产儿脑病,这是脑瘫、认知延迟和行为障碍的主要原因。目前的干预措施有限,没有一种方法被证明可以逆转认知和行为障碍,而这些障碍是这些儿童生活质量差的主要决定因素。此外,导致成熟大脑功能缺陷和影像学异常的围产期脑损伤机制尚未得到明确界定,限制了将干预措施针对那些可能受益最大的人群的潜力。为了确定产前损伤后是否存在损伤可逆性,我们研究了年轻成年动物的一系列功能缺陷和弥散张量成像(DTI)异常。我们假设产前短暂全身缺氧缺血(TSHI)会导致多种功能缺陷,同时伴有微观结构白质和灰质完整性降低,并测试了这些异常是否可以通过产后促红细胞生成素(EPO)来改善,EPO 是一种新兴的神经修复干预措施。在胚胎第 18 天,通过剖腹术短暂地阻塞子宫动脉 60 分钟。假手术组接受麻醉和剖腹术 60 分钟。分娩后,TSHI 幼仔随机接受腹腔内注射 EPO 或载体,从产后第 1 天至第 5 天。在大脑进行离体 DTI 测量分数各向异性、轴向弥散度和径向弥散度之前,从产后第 25-35 天进行步态、社会互动、嗅觉和旷场测试。产前 TSHI 损伤导致年轻成年大鼠出现多动、步态障碍和社交互动能力差,这些缺陷与早产儿出生时观察到的缺陷谱相类似。总的来说,这些数据首次在早产儿脑病模型中表明,产后 EPO 治疗除了步态缺陷外,还可以减轻社交互动障碍。EPO 还使 TSHI 诱导的分数各向异性和径向弥散度的微观结构异常正常化,这与结构完整性的改善和髓鞘形成的恢复一致。总之,这些结果表明围产期脑损伤引起的行为和记忆缺陷是可逆的。此外,DTI 异常的解决可能预示着对新兴干预措施的反应性,并可作为中枢神经系统损伤和恢复的生物标志物。