Cook Children's Medical Center, Fort Worth, TX.
Alexion Pharmaceuticals, Inc., New Haven, CT.
J Clin Lipidol. 2018 May-Jun;12(3):604-614. doi: 10.1016/j.jacl.2018.02.020. Epub 2018 Mar 9.
Measures of atherogenic cholesterol, with and without concomitant use of lipid-lowering medications (LLMs), are reported with up to 52 weeks of sebelipase alfa treatment in children and adults with lysosomal acid lipase deficiency (LAL-D) participating in the phase 3 Acid Lipase Replacement Investigating Safety and Efficacy study (NCT01757184).
To examine the effects of sebelipase alfa on levels of atherogenic biomarkers in the Acid Lipase Replacement Investigating Safety and Efficacy study.
Data were prospectively collected for LDL particle (LDL-P) number, LDL-C, HDL-C, apolipoprotein B (apoB), apolipoprotein A1 (apoA1), and LDL-P size. Differences at week 20 between the sebelipase alfa and placebo groups were assessed for the overall LAL-D cohort and for patients receiving and not receiving LLMs. Changes from baseline after up to 52 weeks of treatment were also calculated for the overall cohort and separately for patients receiving and not receiving LLMs.
Baseline values for LDL-C, LDL-P number, and apoB were elevated while HDL-C and apoA1 were low. Treatment with sebelipase alfa for 20 weeks significantly improved atherogenic measures compared with placebo irrespective of LLM usage. The reduction in LDL-C with sebelipase alfa was associated with a reduction in the LDL-P number. Treatment for up to 52 weeks was associated with sustained improvements of LDL-P, LDL-C, HDL-C, apoB, and apoA1, regardless of LLM use.
Patients with LAL-D have high atherogenic risk. It is essential to address the underlying LAL deficiency to restore cholesterol homeostasis in LAL-D patients, as treatment with sebelipase alfa improves atherogenic measures regardless of LLM use and for a sustained period. Sebelipase alfa appears to reduce LDL-C by decreasing the LDL-P number, suggesting improvement in cardiovascular disease risk in LAL-D patients.
在接受伴有或不伴有降脂药物(LLM)治疗的为期 52 周的贝前列素治疗后,有报道称患有溶酶体酸性脂肪酶缺乏症(LAL-D)的儿童和成人的致动脉粥样硬化胆固醇的水平有所改善,这些患者参与了 3 期酸性脂肪酶替代研究安全性和疗效研究(NCT01757184)。
在酸性脂肪酶替代研究安全性和疗效研究中,研究贝前列素对致动脉粥样硬化生物标志物水平的影响。
前瞻性收集 LDL 颗粒(LDL-P)数量、LDL-C、HDL-C、载脂蛋白 B(apoB)、载脂蛋白 A1(apoA1)和 LDL-P 大小的数据。在整个 LAL-D 队列中,以及在接受和不接受 LLM 的患者中,评估第 20 周时贝前列素组和安慰剂组之间的差异。还计算了整个队列和接受和不接受 LLM 的患者在治疗 52 周后的变化。
LDL-C、LDL-P 数量和 apoB 的基线值升高,而 HDL-C 和 apoA1 的值较低。与安慰剂相比,接受贝前列素治疗 20 周后,致动脉粥样硬化指标明显改善,与 LLM 使用无关。贝前列素降低 LDL-C 与 LDL-P 数量减少有关。接受长达 52 周的治疗与 LDL-P、LDL-C、HDL-C、apoB 和 apoA1 的持续改善相关,与 LLM 的使用无关。
患有 LAL-D 的患者具有高动脉粥样硬化风险。必须解决潜在的 LAL 缺乏症,以恢复 LAL-D 患者的胆固醇稳态,因为贝前列素的治疗无论是否使用 LLM,都能持续改善致动脉粥样硬化指标。贝前列素似乎通过降低 LDL-P 数量来降低 LDL-C,这表明 LAL-D 患者的心血管疾病风险得到了改善。