Safari-Arababadi Amin, Behjati-Ardakani Mostafa, Kalantar Seyed Mehdi, Jaafarinia Mojtaba
Department of Molecular Genetics, Fars Science and Research Branch, Islamic Azad University, Shiraz, Iran.
Yazd Cardiovascular Research Center, Shahid Sadoughi University of Medical Sciences, Yazd, Iran.
Cell Mol Biol (Noisy-le-grand). 2018 Mar 31;64(4):103-107.
JAG1 gene through Notch signaling is implicated in cell fate decisions in early cardiac development, and mutations in several proteins in the pathway have been involved in various disorders. Tetralogy of Fallot (TOF) is the most frequent form of complicated congenital heart disease. The abnormality of TOF begins through the first eight weeks of fetal growth and is confused with ventricular septal defects, obstruction to right ventricular outflow tract, aortic dextroposition, and right ventricular hypertrophy. Hence the existence of mutations in JAG1 gene in Iranian patients with TOF is evaluated. The clinical data and peripheral blood samples were collected from 44 sporadic nonsyndromic patients with TOF and compared to 44 healthy individuals. DNA was extracted, and the exon 6 of the JAG1 gene was amplified by PCR then the PCR products were purified and sequenced. The age range in patients and the control group was 2-36 years, and the mean and standard deviation (SD) of the age in patients was (11.69 ± 7.85 years) and in control group (11.63 ± 7.99 years). Finally, the samples were successfully sequenced, then analyzed and one synonymous variant (c.765C>T; p.Y255Y) was observed in 38 patients with frequency (86.4%) and three controls with frequency (6.8%). The c.765C>T variant is significantly associated with the pathogenesis of TOF in Iranian population.
JAG1基因通过Notch信号通路参与早期心脏发育中的细胞命运决定,该通路中几种蛋白质的突变与多种疾病有关。法洛四联症(TOF)是最常见的复杂先天性心脏病形式。TOF的异常始于胎儿生长的前八周,易与室间隔缺损、右心室流出道梗阻、主动脉右旋和右心室肥厚相混淆。因此,对伊朗TOF患者中JAG1基因的突变情况进行了评估。收集了44例散发非综合征性TOF患者的临床资料和外周血样本,并与44名健康个体进行比较。提取DNA,通过聚合酶链反应(PCR)扩增JAG1基因的第6外显子,然后对PCR产物进行纯化和测序。患者和对照组的年龄范围为2至36岁,患者年龄的平均值和标准差分别为(11.69±7.85岁)和对照组(11.63±7.99岁)。最后,样本成功测序,然后进行分析,在38例患者中观察到一个同义变异(c.765C>T;p.Y255Y),频率为(86.4%),在3名对照中频率为(6.8%)。c.765C>T变异与伊朗人群中TOF的发病机制显著相关。