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对一名患有X染色体缺失的男性患者DNA中缺失的DNA片段进行特异性克隆。

Specific cloning of DNA fragments absent from the DNA of a male patient with an X chromosome deletion.

作者信息

Kunkel L M, Monaco A P, Middlesworth W, Ochs H D, Latt S A

出版信息

Proc Natl Acad Sci U S A. 1985 Jul;82(14):4778-82. doi: 10.1073/pnas.82.14.4778.

DOI:10.1073/pnas.82.14.4778
PMID:2991893
原文链接:https://pmc.ncbi.nlm.nih.gov/articles/PMC390988/
Abstract

A method that allows the specific cloning of DNA fragments absent from patients homozygous or hemizygous for chromosomal deletions is described. The method involves phenol-accelerated competitive DNA reassociation and subsequent molecular cloning of appropriately reassociated molecules. The deletion DNA sample utilized in the competition was isolated from a patient with a minute interstitial deletion in the short arm of the X chromosome. Sheared DNA isolated from a male child, who was diagnosed as having Duchenne muscular dystrophy, chronic granulomatous disease, and retinitis pigmentosa, was combined in a 200-fold excess with Mbo I-cleaved DNA isolated from a 49, XXXXY human lymphoid cell line, and the mixture was subjected to a phenol-enhanced reassociation technique. Analysis of 81 unique segments derived from cloned reassociated DNA molecules has led to the identification of 4 (5%) human DNA fragments that are absent from the male patient's DNA. The 4 clones were localized, on the basis of hybridization with restriction nuclease-digested genomic DNA from a panel of human and human-rodent hybrid cell lines, into three regions surrounding band 21 of the short arm of the normal human X chromosome. These clones are potential linkage markers for the diseases affecting this boy. Each clone, as well as others obtainable by this approach, may also serve as a starting point in the eventual cloning of these three X-linked-disease loci. Extension of this approach to other loci, including human tumors potentially homozygous for small deletions, should also be possible.

摘要

本文描述了一种方法,可用于特异性克隆染色体缺失的纯合或半合子患者所缺失的DNA片段。该方法包括苯酚加速的竞争性DNA复性以及随后对适当复性分子的分子克隆。竞争中使用的缺失DNA样本取自一名X染色体短臂存在微小间隙缺失的患者。将从一名被诊断患有杜氏肌营养不良症、慢性肉芽肿病和色素性视网膜炎的男童中分离的剪切DNA,与从一个49,XXXXY人淋巴母细胞系中分离的经Mbo I酶切的DNA以200倍过量混合,然后对该混合物进行苯酚增强的复性技术处理。对从克隆的复性DNA分子衍生的81个独特片段的分析,已鉴定出4个(5%)在男性患者DNA中不存在的人类DNA片段。根据与一组人和人-鼠杂交细胞系的限制性核酸酶消化的基因组DNA杂交的结果,将这4个克隆定位到正常人类X染色体短臂21带周围的三个区域。这些克隆是影响该男孩疾病的潜在连锁标记。每个克隆以及通过这种方法可获得的其他克隆,也可作为最终克隆这三个X连锁疾病基因座的起点。将这种方法扩展到其他基因座,包括可能因小缺失而纯合的人类肿瘤,应该也是可行的。

https://cdn.ncbi.nlm.nih.gov/pmc/blobs/6b1f/390988/ac77c849f067/pnas00354-0225-a.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/6b1f/390988/b85a580d052e/pnas00354-0224-a.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/6b1f/390988/ac77c849f067/pnas00354-0225-a.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/6b1f/390988/b85a580d052e/pnas00354-0224-a.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/6b1f/390988/ac77c849f067/pnas00354-0225-a.jpg

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Specific cloning of DNA fragments absent from the DNA of a male patient with an X chromosome deletion.对一名患有X染色体缺失的男性患者DNA中缺失的DNA片段进行特异性克隆。
Proc Natl Acad Sci U S A. 1985 Jul;82(14):4778-82. doi: 10.1073/pnas.82.14.4778.
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本文引用的文献

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An (X;11) translocation in a girl with Duchenne muscular dystrophy. Repository identification No. GM1695.一名患有杜氏肌营养不良症女孩的(X;11)易位。储存库识别号GM1695。
Cytogenet Cell Genet. 1980;27(4):268. doi: 10.1159/000131496.
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Isolation and characterization of cloned DNA sequences that hybridize to the human X chromosome.与人类X染色体杂交的克隆DNA序列的分离与鉴定
Cell. 1980 Aug;21(1):95-102. doi: 10.1016/0092-8674(80)90117-8.
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Fertility in patients with X chromosome deletions.
基于长读测序技术的两种 DMD 家系大片段倒位突变的鉴定和特征分析。
Eur J Hum Genet. 2023 May;31(5):504-511. doi: 10.1038/s41431-022-01190-y. Epub 2022 Oct 5.
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A Comprehensive Analysis of 2013 Dystrophinopathies in China: A Report From National Rare Disease Center.中国2013年肌营养不良症综合分析:来自国家罕见病中心的报告
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"Betwixt Mine Eye and Heart a League Is Took": The Progress of Induced Pluripotent Stem-Cell-Based Models of Dystrophin-Associated Cardiomyopathy.“在我的眼与心之间有一个联盟被建立”:基于诱导多能干细胞的肌营养不良相关心肌病模型的进展。
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The discovery of dystrophin, the protein product of the Duchenne muscular dystrophy gene.肌营养不良蛋白的发现,该蛋白是杜氏肌营养不良症基因的产物。
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Caudal epidural block instead of general anesthesia in an adult with Duchenne muscular dystrophy.杜氏肌营养不良症成年患者采用骶管硬膜外阻滞而非全身麻醉。
Local Reg Anesth. 2018 Oct 15;11:75-80. doi: 10.2147/LRA.S180867. eCollection 2018.
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The golden retriever model of Duchenne muscular dystrophy.杜兴氏肌营养不良症的金毛猎犬模型。
Skelet Muscle. 2017 May 19;7(1):9. doi: 10.1186/s13395-017-0124-z.
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GRMD cardiac and skeletal muscle metabolism gene profiles are distinct.杜兴氏型肌营养不良症的心脏和骨骼肌代谢基因谱是不同的。
BMC Med Genomics. 2017 Apr 8;10(1):21. doi: 10.1186/s12920-017-0257-2.
10
Mechanism of Deletion Removing All Dystrophin Exons in a Canine Model for DMD Implicates Concerted Evolution of X Chromosome Pseudogenes.犬类杜氏肌营养不良症模型中删除所有抗肌萎缩蛋白外显子的机制表明X染色体假基因的协同进化。
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Chromosome 15 abnormalities and the Prader-Willi syndrome: a follow-up report of 40 cases.15号染色体异常与普拉德-威利综合征:40例随访报告
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Plasmid screening at high colony density.高菌落密度下的质粒筛选
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Expression of an X-linked gene from an inactive human X chromosome in mouse-human hybrid cells: further evidence for the noninactivation of the steroid sulfatase locus in man.人类X染色体失活状态下X连锁基因在人-鼠杂交细胞中的表达:关于人类类固醇硫酸酯酶基因座未失活的进一步证据
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Identification and isolation of transcribed human X chromosome DNA sequences.转录的人类X染色体DNA序列的鉴定与分离
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