Kunkel L M, Monaco A P, Middlesworth W, Ochs H D, Latt S A
Proc Natl Acad Sci U S A. 1985 Jul;82(14):4778-82. doi: 10.1073/pnas.82.14.4778.
A method that allows the specific cloning of DNA fragments absent from patients homozygous or hemizygous for chromosomal deletions is described. The method involves phenol-accelerated competitive DNA reassociation and subsequent molecular cloning of appropriately reassociated molecules. The deletion DNA sample utilized in the competition was isolated from a patient with a minute interstitial deletion in the short arm of the X chromosome. Sheared DNA isolated from a male child, who was diagnosed as having Duchenne muscular dystrophy, chronic granulomatous disease, and retinitis pigmentosa, was combined in a 200-fold excess with Mbo I-cleaved DNA isolated from a 49, XXXXY human lymphoid cell line, and the mixture was subjected to a phenol-enhanced reassociation technique. Analysis of 81 unique segments derived from cloned reassociated DNA molecules has led to the identification of 4 (5%) human DNA fragments that are absent from the male patient's DNA. The 4 clones were localized, on the basis of hybridization with restriction nuclease-digested genomic DNA from a panel of human and human-rodent hybrid cell lines, into three regions surrounding band 21 of the short arm of the normal human X chromosome. These clones are potential linkage markers for the diseases affecting this boy. Each clone, as well as others obtainable by this approach, may also serve as a starting point in the eventual cloning of these three X-linked-disease loci. Extension of this approach to other loci, including human tumors potentially homozygous for small deletions, should also be possible.
本文描述了一种方法,可用于特异性克隆染色体缺失的纯合或半合子患者所缺失的DNA片段。该方法包括苯酚加速的竞争性DNA复性以及随后对适当复性分子的分子克隆。竞争中使用的缺失DNA样本取自一名X染色体短臂存在微小间隙缺失的患者。将从一名被诊断患有杜氏肌营养不良症、慢性肉芽肿病和色素性视网膜炎的男童中分离的剪切DNA,与从一个49,XXXXY人淋巴母细胞系中分离的经Mbo I酶切的DNA以200倍过量混合,然后对该混合物进行苯酚增强的复性技术处理。对从克隆的复性DNA分子衍生的81个独特片段的分析,已鉴定出4个(5%)在男性患者DNA中不存在的人类DNA片段。根据与一组人和人-鼠杂交细胞系的限制性核酸酶消化的基因组DNA杂交的结果,将这4个克隆定位到正常人类X染色体短臂21带周围的三个区域。这些克隆是影响该男孩疾病的潜在连锁标记。每个克隆以及通过这种方法可获得的其他克隆,也可作为最终克隆这三个X连锁疾病基因座的起点。将这种方法扩展到其他基因座,包括可能因小缺失而纯合的人类肿瘤,应该也是可行的。