Lotlikar Priti P, Creanga Adriana G, Singer Steven R
Division of Oral and Maxillofacial Radiology, Department of Diagnostic Sciences, Rutgers School of Dental Medicine, Newark, New Jersey, USA.
BMJ Case Rep. 2018 Nov 12;2018:bcr-2018-226671. doi: 10.1136/bcr-2018-226671.
Cleidocranial dysplasia (CCD) is a rare congenital autosomal dominant condition, causing hypoplasia of the clavicle, abnormal formation of teeth, skeletal and craniofacial bones. CCD is caused by the mutation of RUNX2/CBFA1 present in the short arm of chromosome 6 at position 21.1, a transcription factor essential for the formation of teeth, cartilage and bone. Patients with CCD show the classical features of excessive mobility of the shoulder bone, lack of resorption of the deciduous teeth, failure to erupt permanent teeth, multiple impacted and supernumerary teeth, and open fontanelle and sutures of the skull. In this article we report a case of CCD in a 16-year-old male patient, with an aim to highlight the clinical, radiological and recommended treatment guidelines.
锁骨颅骨发育不全(CCD)是一种罕见的先天性常染色体显性疾病,可导致锁骨发育不全、牙齿、骨骼和颅面骨形成异常。CCD是由位于6号染色体短臂21.1位置的RUNX2/CBFA1基因突变引起的,RUNX2/CBFA1是一种对牙齿、软骨和骨骼形成至关重要的转录因子。CCD患者具有典型特征,包括肩胛骨活动过度、乳牙未吸收、恒牙萌出失败、多颗阻生牙和多生牙,以及前囟和颅骨缝未闭合。在本文中,我们报告了一例16岁男性CCD患者,旨在强调其临床、影像学表现及推荐的治疗指南。