Abbass Khurram, Krug Hollis
Department of Medicine, Regional Medical Center, San Jose, California, USA.
Rheumatology (111R), Minneapolis VA HCS, Minneapolis, Minnesota, USA.
BMJ Case Rep. 2019 Mar 14;12(3):e226280. doi: 10.1136/bcr-2018-226280.
Granulomatosis with polyangiitis (GPA) was diagnosed in a patient with a 16-month history of IgG4-related lung disease that spontaneously became asymptomatic. Cytoplasmic antineutrophil cytoplasmic antibody (ANCA) was positive at the time of diagnosis of IgG4-related disease (IgG4-RD), but there was no vasculitis or kidney disease. Sixteen months later he developed rapidly progressive glomerulonephritis that responded to cyclophosphamide treatment. While undergoing treatment for GPA, he was found to have a lung mass identified as small cell lung cancer. This mass was present at the time of the IgG4-RD diagnosis. GPA can be confused with IgG4-RD histologically and they rarely coexist. ANCA antibodies are primarily IgG4 subclass. IgG4-RD has been associated with cancer and may improve prognosis. We speculate that this patient may have had small cell lung cancer that incited an IgG4 predominant immune response with coexistent ANCA antibodies that eventually resulted in GPA. Immunosuppressive treatment of GPA likely accelerated the progression of the lung cancer.
一名患有16个月IgG4相关性肺病病史且已自发无症状的患者被诊断为肉芽肿性多血管炎(GPA)。在诊断IgG4相关性疾病(IgG4-RD)时,胞浆抗中性粒细胞胞浆抗体(ANCA)呈阳性,但当时并无血管炎或肾脏疾病。16个月后,他发展为快速进行性肾小球肾炎,对环磷酰胺治疗有反应。在接受GPA治疗期间,他被发现有一个肺部肿块,经鉴定为小细胞肺癌。这个肿块在IgG4-RD诊断时就已存在。GPA在组织学上可能与IgG4-RD混淆,且它们很少共存。ANCA抗体主要是IgG4亚类。IgG4-RD与癌症有关,可能改善预后。我们推测该患者可能患有小细胞肺癌,引发了以IgG4为主的免疫反应,并伴有共存的ANCA抗体,最终导致了GPA。GPA的免疫抑制治疗可能加速了肺癌的进展。