Prasertsan Pharsai, Anuntaseree Wanaporn, Ruangnapa Kanokpan, Saelim Kantara
Department of Pediatrics, Faculty of Medicine, Prince of Songkla University, Songkhla, Thailand.
BMJ Case Rep. 2019 Jul 10;12(7):e228987. doi: 10.1136/bcr-2018-228987.
We report the case of an 8-year-old boy with diffuse large B cell lymphoma who developed a right-sided spontaneous pneumothorax with pleural effusion after recovery from septic shock. The pleural fluid was thought to be malignancy-associated chylothorax concomitant with complicated pleural effusion due to a milky-like appearance, a high level of triglycerides and Gram-negative bacteria staining in the fluid. He was put on total parental nutrition and octreotide for 2 weeks, but did not improve. The laboratory results also showed a persistent bacterial infection in the pleural fluid despite appropriate antibiotics. Eventually, a CT scan revealed a fistulous tract between the right pleural cavity and the stomach. Fistula repair was successful by right open thoracotomy with decortication. Even though the gastropleural fistula is a very rare condition in paediatric patients, the physician should consider this diagnosis in a patient who has an unusual presentation or refractory chylothorax-like pleural effusion.
我们报告了一例8岁弥漫性大B细胞淋巴瘤男孩的病例,该男孩在感染性休克恢复后出现右侧自发性气胸伴胸腔积液。胸腔积液被认为是与恶性肿瘤相关的乳糜胸,并伴有复杂的胸腔积液,因其外观呈乳白色、甘油三酯水平高且积液中革兰氏阴性菌染色阳性。他接受了两周的全胃肠外营养和奥曲肽治疗,但病情并未改善。实验室结果还显示,尽管使用了适当的抗生素,胸腔积液中仍存在持续性细菌感染。最终,CT扫描显示右侧胸腔与胃之间存在瘘管。通过右侧开胸剥脱术成功修复了瘘管。尽管胃胸膜瘘在儿科患者中非常罕见,但对于有异常表现或难治性乳糜胸样胸腔积液的患者,医生应考虑这一诊断。