Takahashi H, Hayashi N, Shibata A
First Department of Internal Medicine, Niigata University School of Medicine, Japan.
Thromb Res. 1988 May 1;50(3):409-18. doi: 10.1016/0049-3848(88)90270-8.
The clinical course and changes in von Willebrand factor (vWf), factor VIII and bleeding time during pregnancy are described in a patient with type IB von Willebrand's disease (vWD) in whom all vWf multimers were present in plasma with relatively reduced content of the high-molecular-weight multimers. At term, ristocetin cofactor was elevated to some extent (from the baseline value of 5 U/dl to 23 U/dl), but never normalized and below the level of vWf antigen (49 U/dl). Bleeding time remained prolonged. In addition, abnormal distribution in the multimer size of plasma vWf was never corrected. These findings contrast with favorable responses during pregnancy reported in type IA individuals. The patient was infused during labor with 400 ml of fresh frozen plasma, and blood loss was approximately 800 ml. Analytical techniques of vWf by crossed immunoelectrophoresis, gel filtration on Sepharose 2B and SDS-agarose gel electrophoresis for the classification of vWD subtypes were compared. Multimer analysis by SDS-agarose gel electrophoresis was needed for differentiation of type IB from type IIA vWD.
本文描述了一名患有IB型血管性血友病(vWD)患者在孕期的临床病程以及血管性血友病因子(vWf)、凝血因子VIII和出血时间的变化情况。该患者血浆中存在所有vWf多聚体,但高分子量多聚体的含量相对减少。足月时,瑞斯托菌素辅因子有所升高(从基线值5 U/dl升至23 U/dl),但从未恢复正常,且低于vWf抗原水平(49 U/dl)。出血时间仍延长。此外,血浆vWf多聚体大小的异常分布从未得到纠正。这些发现与IA型患者孕期的良好反应形成对比。该患者在分娩时输注了400 ml新鲜冰冻血浆,失血量约为800 ml。比较了用于血管性血友病(vWD)亚型分类的交叉免疫电泳、Sepharose 2B凝胶过滤和SDS-琼脂糖凝胶电泳等vWf分析技术。通过SDS-琼脂糖凝胶电泳进行多聚体分析对于区分IB型和IIA型vWD是必要的。