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成人中枢神经系统朗格汉斯细胞组织细胞增多症

Adult Langerhans cell histiocytosis of the central nervous system.

作者信息

Duarte-Celada Walter R, Thakolwiboon Smathorn, Brandi Luis, Duarte-Celada Christopher, Avila Mirla

机构信息

Department of Neurology, Texas Tech University Health Sciences Center, Lubbock, Texas.

Department of Pathology, Texas Tech University Health Sciences Center, Lubbock, Texas.

出版信息

Proc (Bayl Univ Med Cent). 2020 Jun 23;33(4):603-605. doi: 10.1080/08998280.2020.1772184.

Abstract

Langerhans cell histiocytosis (LCH), a disorder characterized by aberrant function and proliferation of mononuclear phagocytic cells called Langerhans cells, usually occurs in those <15 years of age. Adult-onset LCH is extremely rare. We present a case of a 35-year-old woman who presented with multiple episodes of confusion, rapidly progressive cognitive decline, and multiple endocrinopathies, including diabetes insipidus. Brain imaging showed a hypothalamic lesion, and biopsy results confirmed the diagnosis of LCH. Given the wide variety of presentations and the multiple differential diagnoses of hypothalamic lesions, it is essential to be aware of this uncommon condition, especially in adults, where it may be underdiagnosed.

摘要

朗格汉斯细胞组织细胞增多症(LCH)是一种以称为朗格汉斯细胞的单核吞噬细胞功能异常和增殖为特征的疾病,通常发生在15岁以下的人群中。成人发病的LCH极为罕见。我们报告一例35岁女性病例,该患者出现多次意识模糊、快速进展的认知功能减退以及多种内分泌疾病,包括尿崩症。脑部影像学检查显示下丘脑病变,活检结果确诊为LCH。鉴于下丘脑病变的表现形式多样且有多种鉴别诊断,认识到这种罕见疾病非常重要,尤其是在成人中,因为它可能未被充分诊断。

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