Department of Population & Quantitative Health Sciences, Case Western Reserve University, 2103 Cornell Rd, Wolstein Research Building Room 1316, Cleveland, OH, 44106, USA.
Department of Psychological Sciences, Case Western Reserve University, Cleveland, OH, USA.
BMC Pediatr. 2020 Nov 13;20(1):519. doi: 10.1186/s12887-020-02421-1.
Childhood apraxia of speech (CAS) is a neurodevelopmental disorder with heterogeneous communication and other comorbid manifestations. While previous studies have characterized speech deficits associated with CAS, few studies have examined variability in reading and language and/or other developmental comorbidities. We sought to identify comorbid subgroups within CAS that could be clinically relevant as well as genetically distinctive.
In a group of 31 children with CAS and 8 controls, we performed hierarchical cluster analysis utilizing measures of articulation, vocabulary, and reading. We also conducted a chart review of the children with CAS to examine other clinical characteristics in these children and their association with subgroup membership.
We identified 3 comorbid subgroups within CAS of varying severity. The high severity subgroup was characterized by poor reading and vocabulary, and the moderate severity subgroup by poor reading and non-word repetition but average vocabulary, compared to the mild severity subgroup. Subgroups were indistinguishable with respect to speech sound production, the hallmark of CAS, all demonstrating poor articulation. Children in the most severe subgroup were more likely to have early problems feeding (p = 0.036).
Children with CAS may potentially be classified into comorbidity groups based on performance on vocabulary and reading measures, providing additional insight into the heterogeneity within CAS with implications for educational interventions.
儿童言语运动障碍(CAS)是一种神经发育障碍,具有异质性的沟通和其他合并症表现。虽然先前的研究已经描述了与 CAS 相关的言语缺陷,但很少有研究检查阅读和语言以及/或其他发育合并症的变异性。我们试图确定 CAS 中的合并亚组,这些亚组在临床上可能是相关的,并且在遗传上是独特的。
在 31 名 CAS 儿童和 8 名对照儿童中,我们利用发音、词汇和阅读测量进行了层次聚类分析。我们还对患有 CAS 的儿童进行了图表审查,以检查这些儿童的其他临床特征及其与亚组成员身份的关系。
我们在 CAS 中确定了 3 个严重程度不同的合并亚组。高严重程度亚组的特征是阅读和词汇量差,中度严重程度亚组的特征是阅读和非单词重复差,但词汇量平均,而轻度严重程度亚组则不同。亚组在言语产生方面无法区分,这是 CAS 的标志,所有亚组都表现出较差的发音。最严重亚组的儿童更有可能有早期喂养问题(p=0.036)。
根据词汇和阅读测量的表现,CAS 儿童可能可以分为合并症组,这为 CAS 内部的异质性提供了更多的见解,对教育干预具有影响。