Cohen D M, Green J G, Miller J, Gorlin R J, Reed J A
University of Nebraska Medical Center College of Dentistry, Lincoln 68583-0740.
Am J Med Genet. 1987 Oct;28(2):311-24. doi: 10.1002/ajmg.1320280208.
Carpenter syndrome (ACPS type II) was first described by Carpenter in 1901. The syndrome consists of acrocephaly, soft tissue syndactyly, brachy- or agenesis mesophalangy of the hands and feet, preaxial polydactyly, congenital heart disease, mental retardation, hypogenitalism, obesity, and umbilical hernia. Here we review the literature on Carpenter syndrome and add 2 affected sibs with marked intrafamilial variability. This review showed that 2 reported variations of Carpenter syndrome, Goodman and Summitt syndromes, actually fall within the clinical spectrum of this disorder. This confirms earlier suggestions of Gorlin (personal communication 1982) and Hall et al [Am J Med Genet 5:423-434, 1980].
卡彭特综合征(II型尖头并指多指综合征)于1901年由卡彭特首次描述。该综合征包括尖头畸形、软组织并指、手足中节指骨短缩或发育不全、拇指多指畸形、先天性心脏病、智力发育迟缓、生殖器发育不全、肥胖和脐疝。在此,我们回顾了关于卡彭特综合征的文献,并增加了2例有明显家族内变异的患病同胞。该综述表明,先前报道的卡彭特综合征的2种变异型,即古德曼综合征和萨米特综合征,实际上属于该疾病的临床谱系。这证实了戈林(1982年个人交流)以及霍尔等人[《美国医学遗传学杂志》5:423 - 434, 1980]早期的推测。