Scemla Benjamin, Duroi Quentin, Duraffour Pierre, Souedan Vaël, Brézin Antoine P
Université de Paris, Centre d'Ophtalmologie de l'Assistance Publique - Hôpitaux de Paris, Hôpital Cochin, 27 rue du faubourg Saint-Jacques, 75014, Paris, France.
Am J Ophthalmol Case Rep. 2020 Dec 19;21:101003. doi: 10.1016/j.ajoc.2020.101003. eCollection 2021 Mar.
We report the case of a 19-year-old patient who presented with an ocular hypotony due to a transscleral filtration through an isolated congenital chorioretinal coloboma in his right eye.
The initial examination showed a decimal best corrected visual acuity (BCVA) decreased to 0.7 and a marked hypotony. A localized infero-nasal chemosis and a conjunctival hyperemia were observed. The fundus examination showed chorioretinal folds and an edematous disc. In the infero-nasal retinal periphery, a chorioretinal coloboma was seen with a full-thickness scleral defect. Ultrasound biomicroscopy showed the area of the coloboma through which the percolation of fluid occurred.
A favorable outcome was observed within 6 weeks and BCVA improved to 1.0 three months later. The intraocular pressure (IOP) increased to 11 mmHg, but the bleb-like filtration could still be seen together with some persistent chorioretinal folds. Ultrasound Biomicroscopy (UBM) imaging was helpful to understand the mechanism of this uncommon complication of a coloboma.
我们报告一例19岁患者,其右眼因孤立性先天性脉络膜视网膜缺损导致经巩膜滤过而出现低眼压。
初次检查显示小数表示的最佳矫正视力(BCVA)降至0.7,眼压显著降低。观察到局部鼻下结膜水肿和结膜充血。眼底检查显示脉络膜视网膜皱褶和视盘水肿。在鼻下视网膜周边部,可见一个脉络膜视网膜缺损,伴有全层巩膜缺损。超声生物显微镜检查显示了发生液体渗漏的缺损区域。
6周内观察到良好的结果,3个月后BCVA提高到1.0。眼压(IOP)升至11 mmHg,但仍可见泡状滤过,同时伴有一些持续性脉络膜视网膜皱褶。超声生物显微镜(UBM)成像有助于理解这种罕见的缺损并发症的机制。