Department of Biology, University of Alabama at Birmingham, Birmingham, AL, USA.
Department of Genetics, School of Medicine, University of Alabama at Birmingham, Birmingham, AL, USA.
Pigment Cell Melanoma Res. 2021 Mar;34(2):179-187. doi: 10.1111/pcmr.12921. Epub 2020 Sep 4.
Pigmentation abnormalities are reported in the spectrum of phenotypes associated with aging and in patients with mitochondrial DNA depletion syndrome (MDS). Yet, a relevant animal model that mimics these effects and would allow us to evaluate the detrimental aspects of mtDNA depletion on melanocyte function has not been described. Here, we characterize the pigmentary changes observed in the ears of a mtDNA-depleter mouse, which phenotypically includes accentuation of the peri-adnexal pseudonetwork, patchy hyper- and hypopigmentation, and reticular pigmentation. Histologically, these mice show increased epidermal pigmentation with patchy distribution, along with increased and highly dendritic melanocytes. These mtDNA-depleter mice mimic aspects of the cutaneous, pigmentary changes observed in humans with age-related senile lentigines as well as MDS. We suggest that this mouse model can serve as a novel resource for future interrogations of how mitochondrial dysfunction contributes to pigmentary skin disorders. The mtDNA-depleter mouse model also serves as a useful tool to identify novel agents capable of treating pigmentary changes associated with age-related mitochondrial dysfunction in humans.
色素异常可见于与衰老相关的表型谱和线粒体 DNA 耗竭综合征 (MDS) 患者中。然而,目前还没有描述出能够模拟这些影响的相关动物模型,从而使我们能够评估 mtDNA 耗竭对黑素细胞功能的有害方面。在这里,我们描述了在 mtDNA 耗竭小鼠耳朵中观察到的色素变化,其表型包括附属物周围假网络的突出、斑片状色素沉着过度和色素减退以及网状色素沉着。组织学上,这些小鼠表现出斑块状分布的表皮色素沉着增加,同时伴有黑色素细胞数量增加和高度树突状。这些 mtDNA 耗竭小鼠模拟了与年龄相关的老年性黑子以及 MDS 患者的皮肤色素变化。我们认为这种小鼠模型可以作为未来研究线粒体功能障碍如何导致色素性皮肤疾病的新资源。mtDNA 耗竭小鼠模型还可以作为一种有用的工具,用于鉴定能够治疗与年龄相关的线粒体功能障碍相关的色素变化的新型药物。