Kim Joon Goon, Kim Hye Ri, You Moon Hyung, Shin Dong Hoon, Choi Jong Soo, Bae Young Kyung
Department of Dermatology, Yeungnam University College of Medicine, Daegu, Korea.
Department of Pathology, Yeungnam University College of Medicine, Daegu, Korea.
Ann Dermatol. 2020 Feb;32(1):53-56. doi: 10.5021/ad.2020.32.1.53. Epub 2019 Dec 27.
Necrobiotic xanthogranuloma (NXG), is a rare multisystem disease that manifests as cutaneous inflammatory lesions, and is commonly associated with lymphoproliferative disease. Diffuse normolipemic plane xanthoma (NX), is also a rare, acquired disease that is often associated with systemic diseases such as lymphoproliferative disease. Both of these diseases have been reported to be associated with monoclonal gammopathy (MG). However, there are few cases in which these diseases co-exist. A 78-year-old female, who had a known case of NX on the neck and axillary area, presented with an asymptomatic erythematous plaque on her left supraclavicular area. Histopathological examination showed lymphoid aggregates, necrobiotic areas, and granulomatous inflammation in the dermis. Numerous foreignbody and Touton type giant cells were noticed. Serum protein immunoelectrophoresis showed an IgG kappa type MG. Lipid profile of the patient was normal. Bone marrow examination showed plasma cell myeloma. Based on these histologic and laboratory results, we diagnosed this lesion as NXG coexisting with NX and multiple myeloma. She was started on treatment with bortezomib and melphalan for multiple myeloma, and high-dose systemic corticosteroid and triamcinolone intralesional injection for the skin lesion. After 3 months of treatment, the NXG skin lesion and MG improved.
坏死性黄色肉芽肿(NXG)是一种罕见的多系统疾病,表现为皮肤炎性病变,通常与淋巴增殖性疾病相关。弥漫性正常血脂性扁平黄瘤(NX)也是一种罕见的后天性疾病,常与淋巴增殖性疾病等全身性疾病相关。据报道,这两种疾病均与单克隆丙种球蛋白病(MG)有关。然而,这两种疾病并存的病例很少。一名78岁女性,颈部和腋窝区域已知患有NX,左锁骨上区域出现无症状红斑斑块。组织病理学检查显示真皮内有淋巴样聚集、坏死区和肉芽肿性炎症。可见大量异物型和图顿型巨细胞。血清蛋白免疫电泳显示为IgG κ型MG。患者血脂正常。骨髓检查显示为浆细胞骨髓瘤。基于这些组织学和实验室检查结果,我们将此病变诊断为NXG与NX及多发性骨髓瘤并存。她开始接受硼替佐米和马法兰治疗多发性骨髓瘤,高剂量全身皮质类固醇和曲安奈德皮损内注射治疗皮肤病变。治疗3个月后,NXG皮肤病变和MG有所改善。