Abeni Damiano, Rotunno Roberta, Diociaiuti Andrea, Giancristoforo Simona, Bonamonte Domenico, Filoni Angela, Schepis Carmelo, Siragusa Maddalena, Neri Iria, Virdi Annalucia, Castiglia Daniele, Zambruno Giovanna, Bodemer Christine, El Hachem May
IDI-IRCCS (Istituto Dermopatico dell'Immacolata-Istituto di Ricovero e Cura a Carattere Scientifico, Dermatological Research Hospital), Via Monti di Creta 104, IT-00167 Rome, Italy.
Acta Derm Venereol. 2021 Jun 22;101(6):adv00477. doi: 10.2340/00015555-3822.
Autosomal recessive congenital ichthyoses (ARCI) are characterized by generalized skin scaling, hyperkeratosis, erythroderma, and disabling features affecting the skin (palmoplantar keratoderma, fissures, pain, itch), eyes, ears, and joints. Disease severity and chronicity, patient disfigurement, and time and costs required for care impose a major burden on quality of life. This multicentre cross-sectional study investigated the impact of ARCI on quality of life of patients and families, using the Dermatology Life Quality Index (DLQI), the Children DLQI (CDLQI) and Family Burden of Ichthyosis (FBI) questionnaires. Disease severity was assessed by a dermatologist. A total of 94 patients were recruited, of whom 52 (55.3%) children. Mean age was 20.1 (median 13.5) years. The mean CDLQI/DLQI score was 7.8, and 21 patients scored >10, indicating a major impairment in quality of life: symptoms, feelings and treatment problems were the most affected domains of quality of life. FBI showed a major repercussion on psychological factors and work. The results of this study highlight the impact of ARCI on specific aspects of patient and family life, underlining the need for psychological support.
常染色体隐性遗传性先天性鱼鳞病(ARCI)的特征为全身性皮肤鳞屑、角化过度、红皮病,以及影响皮肤(掌跖角化病、皲裂、疼痛、瘙痒)、眼睛、耳朵和关节的致残性特征。疾病的严重程度和慢性病程、患者的容貌毁损以及护理所需的时间和费用对生活质量造成了重大负担。这项多中心横断面研究使用皮肤病生活质量指数(DLQI)、儿童皮肤病生活质量指数(CDLQI)和鱼鳞病家庭负担(FBI)问卷,调查了ARCI对患者及其家庭生活质量的影响。由皮肤科医生评估疾病严重程度。共招募了94名患者,其中52名(55.3%)为儿童。平均年龄为20.1岁(中位数13.5岁)。CDLQI/DLQI平均得分为7.8分,21名患者得分>10分,表明生活质量受到严重损害:症状、感受和治疗问题是生活质量受影响最大的方面。FBI显示对心理因素和工作有重大影响。这项研究的结果突出了ARCI对患者和家庭生活特定方面的影响,强调了心理支持的必要性。