Brito-Zerón Pilar, Pérez-Alvarez Roberto, Feijoo-Massó Carles, Gracia-Tello Borja, González-García Andres, Gómez-de-la-Torre Ricardo, Alguacil Ana, López-Dupla Miguel, Robles Angel, Garcia-Morillo Salvador, Bonet Mariona, Cruz-Caparrós Gracia, Fonseca-Aizpuru Eva, Akasbi Miriam, Callejas Jose Luis, de Miguel-Campo Borja, Pérez-de-Lis Marta, Ramos-Casals Manuel
Systemic Autoimmune Diseases Unit, Hospital CIMA-Sanitas, Barcelona, Spain.
Department of Internal Medicine, Hospital Alvaro Cunqueiro, Vigo, Spain.
Joint Bone Spine. 2021 Dec;88(6):105236. doi: 10.1016/j.jbspin.2021.105236. Epub 2021 Jun 8.
To analyze whether immune-mediated diseases (IMDs) occurs in sarcoidosis more commonly than expected in the general population, and how concomitant IMDs influence the clinical presentation of the disease.
We searched for coexisting IMDs in patients included in the SARCOGEAS-cohort, a multicenter nationwide database of consecutive patients diagnosed according to the ATS/ESC/WASOG criteria. Comparisons were made considering the presence or absence of IMD clustering, and odds ratios (OR) and their 95% confidence intervals (CI) were calculated as the ratio of observed cases of every IMD in the sarcoidosis cohort to the observed cases in the general population.
Among 1737 patients with sarcoidosis, 283 (16%) patients presented at least one associated IMD. These patients were more commonly female (OR: 1.98, 95% CI: 1.49-2.62) and were diagnosed with sarcoidosis at an older age (49.6 vs. 47.5years, P<0.05). The frequency of IMDs in patients with sarcoidosis was nearly 2-fold higher than the frequency observed in the general population (OR: 1.64, 95% CI: 1.44-1.86). Significant associations were identified in 17 individual IMDs. In comparison with the general population, the IMDs with the strongest strength of association with sarcoidosis (OR>5) were common variable immunodeficiency (CVID) (OR: 431.8), familial Mediterranean fever (OR 33.9), primary biliary cholangitis (OR: 16.57), haemolytic anemia (OR: 12.17), autoimmune hepatitis (OR: 9.01), antiphospholipid syndrome (OR: 8.70), immune thrombocytopenia (OR: 8.43), Sjögren syndrome (OR: 6.98), systemic sclerosis (OR: 5.71), ankylosing spondylitis (OR: 5.49), IgA deficiency (OR: 5.07) and psoriatic arthritis (OR: 5.06). Sex-adjusted ORs were considerably higher than crude ORs for eosinophilic digestive disease in women, and for immune thrombocytopenia, systemic sclerosis and autoimmune hepatitis in men.
We found coexisting IMDs in 1 out of 6 patients with sarcoidosis. The strongest associations were found for immunodeficiencies and some systemic, rheumatic, hepatic and hematological autoimmune diseases.
分析结节病患者中免疫介导疾病(IMDs)的发生是否比普通人群更常见,以及合并的IMDs如何影响该疾病的临床表现。
我们在SARCOGEAS队列研究纳入的患者中搜索并存的IMDs,该队列是一个全国多中心数据库,纳入了根据美国胸科学会(ATS)/欧洲呼吸学会(ESC)/世界结节病和其他肉芽肿病协会(WASOG)标准诊断的连续患者。根据是否存在IMD聚集进行比较,并计算比值比(OR)及其95%置信区间(CI),作为结节病队列中每种IMD的观察病例数与普通人群中观察病例数的比值。
在1737例结节病患者中,283例(16%)患者至少合并一种相关的IMD。这些患者女性更为常见(OR:1.98,95%CI:1.49-2.62),且诊断结节病时年龄较大(49.6岁对47.5岁,P<0.05)。结节病患者中IMDs的发生率比普通人群中观察到的发生率高近2倍(OR:1.64,95%CI:1.44-1.86)。在17种个体IMD中发现了显著关联。与普通人群相比,与结节病关联强度最强(OR>5)的IMDs是常见可变免疫缺陷(CVID)(OR:431.8)、家族性地中海热(OR:33.9)、原发性胆汁性胆管炎(OR:16.57)、溶血性贫血(OR:12.17)、自身免疫性肝炎(OR:9.01)、抗磷脂综合征(OR:8.70)、免疫性血小板减少症(OR:8.43)、干燥综合征(OR:6.98)、系统性硬化症(OR:5.71)、强直性脊柱炎(OR:5.49)、IgA缺乏症(OR:5.07)和银屑病关节炎(OR:5.06)。女性嗜酸性消化疾病以及男性免疫性血小板减少症、系统性硬化症和自身免疫性肝炎的性别调整OR值明显高于粗OR值。
我们发现每6例结节病患者中有1例并存IMDs。免疫缺陷以及一些全身性、风湿性、肝脏和血液系统自身免疫性疾病的关联最为显著。