Department of Ophthalmology, IRCCS San Raffaele Scientific Insititute, via Olgettina 60, 20132, Milan, Italy.
Sci Rep. 2021 Jul 19;11(1):14735. doi: 10.1038/s41598-021-94310-5.
Outer retinal tubulations (ORT) are a relatively new finding characterizing outer retinal atrophy. The main aim of the present study was to describe ORT development in advanced age-related macular degeneration (AMD) and to assess its relationship with disease's severity. Patients with advanced AMD characterized either by macular neovascularization or geographic atrophy, showing signs of outer retinal disruption or retinal pigment epithelium atrophy on structural optical coherence tomography (OCT) at the inclusion examination were prospectively recruited. All the patients underwent complete ophthalmologic evaluation, structural OCT scans and fundus autofluorescence imaging. The planned follow-up was of 3-years. Main outcome measures were ORT prevalence, mechanism of ORT formation, mean time needed for complete ORT formation, best-corrected visual acuity (BCVA), definitely decreased autofluorescence (DDAF) area, questionably decreased autofluorescence (QDAF) area, retinal layer thickness, foveal sparing, number of intravitreal injections. We also assessed the possible role of external limiting membrane (ELM) and Müller cells in ORT pathogenesis. Seventy eyes (70 patients) were included; 43 showed dry AMD evolving to geographic atrophy, while 27 displayed the features of wet AMD. Baseline BCVA was 0.5 ± 0.5 LogMAR, decreasing to 0.9 ± 0.5 LogMAR at the 3-year follow-up (p < 0.01). We detected completely formed ORT in 26/70 eyes (37%), subdivided as follows: 20 eyes (77%) wet AMD and 6 eyes (23%) dry AMD (p < 0.01). ORT took 18 ± 8 months (range 3-35 months) to develop fully. We described the steps leading to ORT development, characterized by progressive involvement of, and damage to the photoreceptors, the ELM and the RPE. Eyes displaying ORT were associated with a smaller QDAF area, less retinal layers damage and lower rate of foveal sparing than eyes free of ORT (p < 0.01). We also described pigment accumulations simulating ORT, which were detected in 16/70 eyes (23%), associated with a greater loss of foveal sparing, increased DDAF area and smaller QDAF area at the 3-year follow-up (p < 0.01). In conclusion, this study provided a description of the steps leading to ORT development in AMD. ELM and Müller cells showed a role in ORT pathogenesis. Furthermore, we described a subtype of pigment hypertrophy mimicking ORT, evaluating its clinical utility.
外视网膜管腔化(ORT)是一种新的特征性表现,可用于描述外视网膜萎缩。本研究的主要目的是描述晚期年龄相关性黄斑变性(AMD)中 ORT 的发展,并评估其与疾病严重程度的关系。在纳入研究时,对表现出外视网膜破坏或视网膜色素上皮萎缩的特征的晚期 AMD 患者(无论是由黄斑新生血管还是地理萎缩引起),使用结构光学相干断层扫描(OCT)进行前瞻性招募。所有患者均接受了全面的眼科评估、结构 OCT 扫描和眼底自发荧光成像。计划的随访时间为 3 年。主要观察指标包括 ORT 的患病率、ORT 形成的机制、完全形成 ORT 所需的平均时间、最佳矫正视力(BCVA)、明确的自发荧光减少区(DDAF)、可疑的自发荧光减少区(QDAF)、视网膜层厚度、黄斑中心凹保留、玻璃体内注射次数。我们还评估了外节层(ELM)和 Müller 细胞在外膜管腔化发病机制中的可能作用。共纳入 70 只眼(70 例患者);43 只眼为干性 AMD 进展为地理萎缩,27 只眼为湿性 AMD。基线时 BCVA 为 0.5±0.5 LogMAR,3 年随访时降至 0.9±0.5 LogMAR(p<0.01)。我们在 26/70 只眼(37%)中检测到完全形成的 ORT,分为以下两种类型:20 只眼(77%)为湿性 AMD,6 只眼(23%)为干性 AMD(p<0.01)。完全形成 ORT 平均需要 18±8 个月(3-35 个月)。我们描述了导致 ORT 发展的步骤,其特征为感光细胞、ELM 和 RPE 的逐渐受累和损伤。与没有 ORT 的眼睛相比,出现 ORT 的眼睛与较小的 QDAF 区、较少的视网膜层损伤和更低的黄斑中心凹保留率相关(p<0.01)。我们还描述了在 16/70 只眼(23%)中发现的模拟 ORT 的色素积聚,这些眼睛在 3 年随访时表现出更大的黄斑中心凹保留丧失、DDAF 区增加和 QDAF 区减少(p<0.01)。总之,本研究对外膜管腔化在 AMD 中的发展步骤进行了描述。ELM 和 Müller 细胞在外膜管腔化发病机制中发挥了作用。此外,我们还描述了一种模拟外膜管腔化的色素肥大亚型,并评估了其临床应用。