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一名15个月大儿童体内存在两个含有脑膜上皮成分的独立毛发状息肉。

Presence of Two Separate Hairy Polyps with Meningothelial Elements in a 15-Month-Old Child.

作者信息

Alghamdi Ahmad Saeed A, Almutairi Nasser, Alokby Ghassan

机构信息

College of Medicine, Taif University, Taif, Saudi Arabia.

Department of Otolaryngology-Head and Neck Surgery, King Faisal Specialist Hospital and Research Centre, Riyadh, Saudi Arabia.

出版信息

Case Rep Otolaryngol. 2021 Sep 21;2021:1844244. doi: 10.1155/2021/1844244. eCollection 2021.

Abstract

Hairy polyps are benign embryological tumors of the head and neck region that are derived from two germinal layers, the ectoderm and mesoderm. At an incidence of 1 : 40000, hairy polyps are considered rare growths. Presenting symptoms of hairy polyps can vary greatly depending on the size and location of the tumor. To the best of our knowledge, our reported case is the first in the literature to highlight an extremely rare occurrence of two separate hairy polyps being simultaneously present in one patient, in the clivus and the nasion, with the presence of meningothelial cells within both tumors, histopathologically. With surgical resection as the management of choice, the approach of surgery differs greatly depending on many factors. Since the patient in our reported case had a cleft palate, we used a combined transnasal and transoral approach to fully release the clival mass and a direct skin incision for the nasion mass. Recurrence after complete surgical resection is rare, and if happens, it should rise suspicion of histopathologically misdiagnosed tumor. We amplified the importance of advanced radiological investigations along with proper multidisciplinary teamwork to exclude CNS connections and other histologically malignant tumors and to early pick up a possible simultaneous lesion.

摘要

毛发状息肉是头颈部的良性胚胎性肿瘤,起源于外胚层和中胚层两个生发层。毛发状息肉的发病率为1∶40000,被认为是罕见的生长物。毛发状息肉的症状表现因肿瘤大小和位置的不同而有很大差异。据我们所知,我们报告的病例是文献中首例突出显示一名患者同时出现两个独立的毛发状息肉,分别位于斜坡和鼻根,且组织病理学显示两个肿瘤内均存在脑膜内皮细胞的极为罕见的病例。手术切除是首选的治疗方法,手术方式因多种因素而有很大不同。由于我们报告病例中的患者患有腭裂,我们采用经鼻和经口联合入路来完全切除斜坡肿物,并通过直接皮肤切口切除鼻根肿物。完全手术切除后复发很少见,如果发生复发,则应怀疑组织病理学误诊的肿瘤。我们强调了先进的放射学检查以及适当的多学科团队协作的重要性,以排除中枢神经系统连接和其他组织学上的恶性肿瘤,并尽早发现可能的同时存在的病变。

https://cdn.ncbi.nlm.nih.gov/pmc/blobs/3ee3/8478528/97ade4125c3a/CRIOT2021-1844244.001.jpg

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