Suppr超能文献

从单纯性大疱性表皮松解症和扩张型心肌病患者中产生两个诱导多能干细胞系,并对与KLHL24翻译起始密码子杂合突变相关的基因进行修复。

Generation and genetic repair of two human induced pluripotent cell lines from patients with Epidermolysis Bullosa simplex and dilated cardiomyopathy associated with a heterozygous mutation in the translation initiation codon of KLHL24.

作者信息

Ramovs Veronika, Fuentes Ignacia, Freund Christian, Mikkers Harald, Mummery Christine L, Raymond Karine

机构信息

Department of Anatomy and Embryology, Leiden University Medical Center, Leiden 2333 ZC, The Netherlands.

Fundación DEBRA Chile, Santiago, Chile; Centro de Genética y Genómica, Facultad de Medicina, Clínica Alemana Universidad del Desarrollo, Santiago, Chile.

出版信息

Stem Cell Res. 2021 Dec;57:102582. doi: 10.1016/j.scr.2021.102582. Epub 2021 Oct 21.

Abstract

Fibroblasts from two patients carrying a heterozygous mutation in the translation initiation codon (c.2 T > G) of the kelch-like protein 24 (KLHL24) gene were used to generate human induced pluripotent stem cells (hiPSCs), using non-integrating Sendai virus to deliver reprogramming factors. CRISPR-Cas9 editing was used for genetic correction of the mutation in the patient-hiPSCs. The top-predicted off-target sites were not altered. Patient and isogenic hiPSCs showed typical morphology, expressed pluripotency-associated markers, had the capacity for in vitro differentiation into the three germ layers and displayed a normal karyotype. These isogenic pairs will enable in vitro modelling of KLHL24-associated heart and skin conditions.

摘要

利用携带kelch样蛋白24(KLHL24)基因翻译起始密码子杂合突变(c.2 T>G)的两名患者的成纤维细胞,通过非整合仙台病毒递送重编程因子来生成人类诱导多能干细胞(hiPSC)。CRISPR-Cas9编辑用于对患者来源的hiPSC中的突变进行基因校正。预测的脱靶位点没有改变。患者来源的hiPSC和同基因hiPSC表现出典型的形态,表达多能性相关标志物,具有体外分化为三个胚层的能力,并且核型正常。这些同基因细胞对将有助于对与KLHL24相关的心脏和皮肤疾病进行体外建模。

文献AI研究员

20分钟写一篇综述,助力文献阅读效率提升50倍。

立即体验

用中文搜PubMed

大模型驱动的PubMed中文搜索引擎

马上搜索

文档翻译

学术文献翻译模型,支持多种主流文档格式。

立即体验