Neurology Unit, Maggiore Della Carità Hospital, Department of Translational Medicine, University of Piemonte Orientale, Ospedale Maggiore Della Carità, via Mazzini 18, Novara, Italy.
Interdisciplinary Research Center of Autoimmune Diseases (IRCAD), Department of Health Sciences, University of Piemonte Orientale, Novara, Italy.
Neurol Sci. 2022 Jun;43(6):3919-3922. doi: 10.1007/s10072-022-05865-8. Epub 2022 Jan 10.
A 35-year-old Caucasian woman presented an abrupt onset of bilateral impaired vision, and arrived to our attention two weeks later. She had a previous episode of mild dizziness. She underwent a fluorescein angiography showing branch retinal artery occlusions and a brain magnetic resonance imaging (MRI) revealing several supraand infratentorial FLAIR-hyperintense white matter lesions, two with contrast enhancement. Thrombophilic, autoimmune and infective (including Human Immunodeficiency Virus, Borrelia burgdorferi, Hepatitis B Virus, Hepatitis C Virus, Herpes Simplex Virus 1-2, Varicella Zoster Virus) screening was negative. Cerebrospinal fluid analysis showed intrathecal IgG synthesis. We suspected a Primary Central Nervous System Vasculitis, and intravenous steroids were started. Three months later a second brain MRI showed seven new lesions without contrast enhancement, and she revealed a cognitive impairment and bilateral hearing loss. Reviewing the clinical history and MRI, she fulfilled diagnostic criteria for Susac syndrome. She had two cycles of cyclophosphamide, and recovered in 6 months and then remained stable with metotrexate.
一位 35 岁的白种女性突发双侧视力受损,两周后到我院就诊。她曾有过一次轻度头晕的发作。她进行了荧光素血管造影检查,显示分支视网膜动脉阻塞,并进行了脑部磁共振成像(MRI)检查,发现多个幕上和幕下 FLAIR 高信号白质病变,其中两个有对比增强。血栓形成倾向、自身免疫和感染(包括人类免疫缺陷病毒、伯氏疏螺旋体、乙型肝炎病毒、丙型肝炎病毒、单纯疱疹病毒 1-2、水痘带状疱疹病毒)筛查均为阴性。脑脊液分析显示鞘内 IgG 合成。我们怀疑是原发性中枢神经系统血管炎,并开始静脉注射类固醇。三个月后,第二次脑部 MRI 显示七个新的无对比增强病变,她出现认知障碍和双侧听力损失。回顾临床病史和 MRI,她符合 Susac 综合征的诊断标准。她接受了两个周期的环磷酰胺治疗,6 个月后康复,然后继续使用甲氨蝶呤治疗,病情稳定。