Li Xiao-Jun, Morgan Charles, Goff Loyal A, Doetzlhofer Angelika
The Solomon H. Snyder Department of Neuroscience, Johns Hopkins University School of Medicine, Baltimore, MD 21205, USA.
McKusick-Nathans Institute for Genetic Medicine, Johns Hopkins University School of Medicine, Baltimore, MD 21205, USA.
Sci Adv. 2022 Feb 11;8(6):eabj7651. doi: 10.1126/sciadv.abj7651.
Hair cell (HC) loss within the inner ear cochlea is a leading cause for deafness in humans. Before the onset of hearing, immature supporting cells (SCs) in neonatal mice have some limited capacity for HC regeneration. Here, we show that in organoid culture, transient activation of the progenitor-specific RNA binding protein LIN28B and Activin antagonist follistatin (FST) enhances regenerative competence of maturing/mature cochlear SCs by reprogramming them into progenitor-like cells. Transcriptome profiling and mechanistic studies reveal that LIN28B drives SC reprogramming, while FST is required to counterbalance hyperactivation of transforming growth factor-β-type signaling by LIN28B. Last, we show that LIN28B and FST coactivation enhances spontaneous cochlear HC regeneration in neonatal mice and that LIN28B may be part of an endogenous repair mechanism that primes SCs for HC regeneration. These findings indicate that SC dedifferentiation is critical for HC regeneration and identify LIN28B and FST as main regulators.
内耳耳蜗中的毛细胞(HC)损失是导致人类耳聋的主要原因。在听力开始之前,新生小鼠中未成熟的支持细胞(SC)具有一定的有限的HC再生能力。在这里,我们表明,在类器官培养中,祖细胞特异性RNA结合蛋白LIN28B和激活素拮抗剂卵泡抑素(FST)的短暂激活通过将成熟/成熟的耳蜗SC重编程为祖细胞样细胞来增强其再生能力。转录组分析和机制研究表明,LIN28B驱动SC重编程,而FST是平衡LIN28B对转化生长因子-β型信号过度激活所必需的。最后,我们表明LIN28B和FST的共同激活增强了新生小鼠耳蜗的自发HC再生,并且LIN28B可能是内源性修复机制的一部分,该机制使SC为HC再生做好准备。这些发现表明SC去分化对HC再生至关重要,并确定LIN28B和FST为主要调节因子。