Division of Hematology, Department of Internal Medicine, Mayo Clinic, MN.
Haematologica. 2022 Jul 1;107(7):1503-1517. doi: 10.3324/haematol.2021.279500.
Chronic myelomonocytic leukemia (CMML) is a myelodysplastic syndrome/myeloproliferative overlap neoplasm characterized by sustained peripheral blood monocytosis and an inherent risk for transformation to acute myeloid leukemia (15-30% over 3-5 years). While CMML is morphologically classified into CMML-0, 1 and 2 based on peripheral blood and bone marrow promonocyte/blast counts, a more clinically relevant classification into dysplastic and proliferative subtypes, based on the presenting white blood cell count, is helpful in prognostication and therapeutics. CMML is a neoplasm associated with aging, occurring on the background of clonal hematopoiesis, with TET2 and SRSF2 mutations being early initiating events. The subsequent acquisitions of ASXL1, RUNX1, SF3B1 and DNMT3A mutations usually give rise to dysplastic CMML, while ASXL1, JAK2V617F and RAS pathway mutations give rise to proliferative CMML. Patients with proliferative CMML have a more aggressive course with higher rates of transformation to acute myeloid leukemia. Allogeneic stem cell transplant remains the only potential cure for CMML; however, given the advanced median age at presentation (73 years) and comorbidities, it is an option for only a few affected patients (10%). While DNA methyltransferase inhibitors are approved for the management of CMML, the overall response rates are 40-50%, with true complete remission rates of <20%. These agents seem to be particularly ineffective in proliferative CMML subtypes with RAS mutations, while the TET2mutant/ASXL1wildtype genotype seems to be the best predictor for responses. These agents epigenetically restore hematopoiesis in responding patients without altering mutational allele burdens and progression remains inevitable. Rationally derived personalized/targeted therapies with disease-modifying capabilities are much needed.
慢性髓单核细胞白血病 (CMML) 是一种骨髓增生异常/骨髓增殖性重叠肿瘤,其特征为外周血单核细胞持续增多,并具有向急性髓系白血病转化的固有风险(3-5 年内为 15-30%)。虽然 CMML 根据外周血和骨髓原始细胞/早幼粒细胞计数分为 CMML-0、1 和 2,但根据初始白细胞计数进行更具临床相关性的增生和发育不良亚型分类有助于预后和治疗。CMML 是一种与衰老相关的肿瘤,发生在克隆性造血的背景下,TET2 和 SRSF2 突变是早期起始事件。随后获得 ASXL1、RUNX1、SF3B1 和 DNMT3A 突变通常会导致发育不良的 CMML,而 ASXL1、JAK2V617F 和 RAS 通路突变会导致增生性 CMML。增生性 CMML 患者病程更具侵袭性,向急性髓系白血病转化的发生率更高。异基因造血干细胞移植仍然是 CMML 的唯一潜在治愈方法;然而,由于发病时的中位年龄(73 岁)较高且合并症较多,仅有少数受影响的患者(10%)可以选择这种方法。尽管 DNA 甲基转移酶抑制剂已被批准用于 CMML 的治疗,但总体缓解率为 40-50%,真正的完全缓解率<20%。这些药物在伴有 RAS 突变的增生性 CMML 亚型中似乎效果不佳,而 TET2 突变/ASXL1 野生型基因型似乎是预测反应的最佳指标。这些药物在不改变突变等位基因负担的情况下使反应患者的造血功能得到重建,进展仍然不可避免。迫切需要具有疾病修饰能力的基于理性设计的个体化/靶向治疗。