Koh Alex Zhi Yang, Nyanti Larry Ellee, Lim Sheri, Luk Tien Loong, Tang Andy Sing Ong, Leong Tze Shin, Chew Lee Ping
Haematology Unit, Department of Internal Medicine, Sarawak General Hospital, Ministry of Health, Sarawak, Malaysia.
Faculty of Medicine and Health Sciences, Universiti Malaysia Sabah, Kota Kinabalu, Malaysia.
Radiol Case Rep. 2022 Apr 22;17(6):2243-2246. doi: 10.1016/j.radcr.2022.03.097. eCollection 2022 Jun.
Trichobezoars are usually formed due to ingestion of hair or hair-like fibres and present with a wide spectrum of clinical manifestations. We report a case of Rapunzel's syndrome associated with trichotillomania in a 16-year-old girl who presented to our Haematology unit with complaints of fatigue, abdominal distention, and early satiety. Initial evaluation demonstrated anaemia, thrombocytosis, and a left hypochondrial mass suggestive of splenomegaly. However, ultrasound of the abdomen showed no hepatosplenomegaly and blood investigations were not suggestive of haematological malignancy. Not long after, the patient presented to the emergency department with suspected acute abdomen. Computed tomography of the abdomen revealed intraluminal gastric and jejunal masses causing small bowel obstruction. Emergency laparotomy confirmed gastric and jejunal trichobezoars, and subsequent psychiatric evaluation confirmed trichotillomania. Clinicians should consider trichobezoar in the differential diagnosis of abdominal pain and a non-tender 'spleen-like' abdominal mass.
毛发石通常是由于摄入毛发或毛发样纤维而形成的,临床表现多种多样。我们报告一例与拔毛癖相关的长发公主综合征,患者为一名16岁女孩,因疲劳、腹胀和早饱感就诊于我院血液科。初步评估显示贫血、血小板增多症以及左季肋部肿块提示脾肿大。然而,腹部超声未显示肝脾肿大,血液检查也未提示血液系统恶性肿瘤。不久后,患者因疑似急腹症就诊于急诊科。腹部计算机断层扫描显示胃和空肠腔内肿块导致小肠梗阻。急诊剖腹探查证实胃和空肠毛发石,随后的精神科评估证实为拔毛癖。临床医生在腹痛和无压痛的“脾样”腹部肿块的鉴别诊断中应考虑毛发石。