Cardiology, Hospital Garcia de Orta EPE, Almada, Setúbal, Portugal.
Cardiology, Hospital Garcia de Orta EPE, Almada, Setúbal, Portugal
BMJ Case Rep. 2022 May 11;15(5):e247070. doi: 10.1136/bcr-2021-247070.
A female patient in her early 30s, with a medical history of pulmonary arterial hypertension associated with congenital heart disease, lost to follow-up, was referred to a pulmonary hypertension reference centre. The patient presented at a WHO functional class of II in a low-risk category. A transthoracic echocardiogram demonstrated severe pulmonary hypertension with right ventricular dysfunction. A cardiac MRI demonstrated a right aortic arch with anomalous origin of the left pulmonary artery from the ascending thoracic aorta and a patent ductus arteriosus. A right heart catheterisation confirmed the presence of severe pulmonary hypertension. The patient was started on combined vasodilator therapy with an improvement in symptoms and remaining in a low-risk category. This represents one of the oldest described cases of such an anomaly and the first description of response to vasodilator therapy, highlighting the importance of a structured approach in a reference centre for achieving optimal outcomes.
一位 30 岁出头的女性患者,有肺动脉高压合并先天性心脏病病史,失访后被转至肺动脉高压诊治中心。患者就诊时为世界卫生组织(WHO)功能分级 II 级、低危组。经胸超声心动图显示严重肺动脉高压合并右心室功能障碍。心脏 MRI 显示右位主动脉弓伴左肺动脉异常起源于升主动脉,动脉导管未闭。右心导管检查证实存在严重肺动脉高压。患者开始接受联合血管扩张剂治疗,症状改善,仍处于低危组。这是该种异常中描述最早的病例之一,也是首例对血管扩张剂治疗有反应的描述,突出了在诊治中心采用结构化方法实现最佳治疗效果的重要性。