Peery W H
Am J Med. 1987 May;82(5):989-97. doi: 10.1016/0002-9343(87)90162-8.
Hereditary hemorrhagic telangiectasia (Osler-Weber-Rendu disease) is an autosomal dominant, systemic fibrovascular dysplasia in which telangiectases, arteriovenous malformations, and aneurysms may be widely distributed throughout the body vasculature. Major clinical manifestations include: recurrent bleeding from mucosal telangiectases and arteriovenous malformations; hypoxemia, cerebral embolism, and brain abscess due to pulmonary arteriovenous fistulas; high-output congestive heart failure and portosystemic encephalopathy from hepatic arteriovenous malformations; and a variety of neurologic symptoms due to central nervous system angiodysplasia. Therapy is primarily supportive, consisting of iron supplementation and blood transfusion. Septal dermoplasty and oral estrogens may allow prolonged remission of epistaxis, but permanent surgical cure of gastrointestinal bleeding is rarely feasible because of diffuse angiodysplasia of the alimentary tract. Ligation, resection, or embolization may be indicated for pulmonary arteriovenous fistulas. The prognosis and survival of patients with hereditary hemorrhagic telangiectasia are favorable, providing treatable complications are accurately diagnosed.
遗传性出血性毛细血管扩张症(奥斯勒-韦伯-伦杜病)是一种常染色体显性全身性纤维血管发育异常疾病,其中毛细血管扩张、动静脉畸形和动脉瘤可能广泛分布于全身脉管系统。主要临床表现包括:黏膜毛细血管扩张和动静脉畸形反复出血;肺动静脉瘘导致的低氧血症、脑栓塞和脑脓肿;肝动静脉畸形引起的高输出量充血性心力衰竭和门体性脑病;以及中枢神经系统血管发育异常导致的各种神经症状。治疗主要是支持性的,包括补充铁剂和输血。鼻中隔植皮术和口服雌激素可能使鼻出血长期缓解,但由于消化道广泛的血管发育异常,很少能通过手术永久治愈胃肠道出血。对于肺动静脉瘘,可能需要进行结扎、切除或栓塞。如果能准确诊断可治疗的并发症,遗传性出血性毛细血管扩张症患者的预后和生存率是良好的。