Department of Neurosurgery, Johns Hopkins University School of Medicine, , 600 N. Wolfe St., Meyer 7-113, Baltimore, MD 21287, USA.
Department of Neurosurgery, Johns Hopkins University School of Medicine, , 600 N. Wolfe St., Meyer 7-113, Baltimore, MD 21287, USA.
Spine J. 2022 Dec;22(12):1944-1952. doi: 10.1016/j.spinee.2022.08.008. Epub 2022 Aug 24.
Ehlers-Danlos syndrome (EDS) is a rare hereditary condition that can result in ligamentous laxity and hypermobility of the cervical spine. A subset of patients can develop clinical instability of the craniocervical junction associated with pain and neurological dysfunction, potentially warranting treatment with occipitocervical fixation (OCF). Surgical decision-making in patients with EDS can be complicated by difficulty distinguishing from hypermobility inherent in the disease and true pathological instability necessitating intervention. Here we comprehensively review the available medical literature to critically appraise the evidence behind various proposed definitions of instability in the EDS population, and summarize the available outcomes data after OCF. Several radiographic parameters have been used, including the clivo-axial angle, basion-axial interval, and pB-C2 measurement. Despite increasing recognition of EDS by spine surgeons, there remains a paucity of data supporting proposed radiographic parameters for spinal instability among EDS patients. Furthermore, there is a lack of high-quality evidence concerning the efficacy of surgical treatments for chronic debilitating pain prevalent in this population. More standardized clinical measures and rigorous study methodologies are needed to elucidate the role of surgical intervention in this complex patient population.
埃勒斯-当洛斯综合征(EDS)是一种罕见的遗传性疾病,可导致颈椎韧带松弛和过度活动。一部分患者可能会出现颅颈交界区的临床不稳定,伴有疼痛和神经功能障碍,可能需要行枕颈固定术(OCF)治疗。EDS 患者的手术决策可能很复杂,因为难以区分疾病固有的过度活动和需要干预的真正病理性不稳定。在这里,我们全面回顾了现有的医学文献,批判性地评估了 EDS 人群中各种不稳定定义背后的证据,并总结了 OCF 后的现有结果数据。已经使用了几种影像学参数,包括寰齿关节角、基底-枢轴间隔和 pB-C2 测量。尽管脊柱外科医生对 EDS 的认识不断提高,但仍缺乏支持 EDS 患者脊柱不稳定的影像学参数的大量数据。此外,对于该人群中普遍存在的慢性致残性疼痛的手术治疗效果,缺乏高质量的证据。需要更标准化的临床措施和严格的研究方法来阐明手术干预在这一复杂患者群体中的作用。