Davidson Aimee L, Kondrashova Olga, Leonard Conrad, Wood Scott, Tudini Emma, Hollway Georgina E, Pearson John V, Newell Felicity, Spurdle Amanda B, Waddell Nicola
QIMR Berghofer Medical Research Institute, Brisbane, Queensland, Australia.
Faculty of Medicine, The University of Queensland, Brisbane, Queensland, Australia.
Hum Mutat. 2022 Dec;43(12):2054-2062. doi: 10.1002/humu.24468. Epub 2022 Oct 2.
The clinical classification of variants may change with new information, however, there is limited guidance on how often significant changes in variant classification occur. We used ClinVar to examine how variant classification changes over time. We developed a custom parser and accessed variant data from ClinVar between January 2015 and July 2021. The ClinVar-assigned "aggregate" classification of variants in 121 hereditary cancer genes was harmonized across releases to align to the American College of Medical Genetics and Genomics and the Association for Molecular Pathology terms. Aggregate classification categories were grouped as: benign/likely benign (B/LB); likely pathogenic/pathogenic (LP/P); variant of uncertain significance (VUS); conflicting interpretations of pathogenicity (Conflicting); or Other. We profiled changes in aggregate variant classification between consecutive semi-annual ClinVar releases. The proportion of variants that changed aggregate classification between semi-annual ClinVar releases ranged from 0.6% to 6.4%. The most frequent changes were "VUS to conflicting," "other to LP/P," and "B/LB to Conflicting." A limited number of variants changed aggregate classification from "LP/P to B/LB," or vice versa. Our analysis indicates need for regular reassessment of clinical variant interpretations. The parser developed for this project will facilitate extraction of relevant interpretation data from ClinVar.
变异的临床分类可能会随着新信息而改变,然而,关于变异分类发生重大变化的频率,目前的指导有限。我们使用ClinVar来研究变异分类如何随时间变化。我们开发了一个自定义解析器,并获取了2015年1月至2021年7月期间ClinVar中的变异数据。对121个遗传性癌症基因变异的ClinVar指定“综合”分类在各版本之间进行了统一,以符合美国医学遗传学与基因组学学会和分子病理学协会的术语。综合分类类别分为:良性/可能良性(B/LB);可能致病/致病(LP/P);意义未明变异(VUS);致病性的相互矛盾解释(相互矛盾);或其他。我们分析了ClinVar连续两个半年发布版本之间综合变异分类的变化。在ClinVar的两个半年发布版本之间,综合分类发生变化的变异比例在0.6%至6.4%之间。最常见的变化是“VUS变为相互矛盾”、“其他变为LP/P”以及“B/LB变为相互矛盾”。只有少数变异的综合分类从“LP/P变为B/LB”,反之亦然。我们的分析表明需要定期重新评估临床变异解释。为该项目开发的解析器将有助于从ClinVar中提取相关解释数据。