Okamura Hiroki, Ishikawa Hiroki, Ohno Takuya, Fujita Shogo, Inagaki Katsunori
Department of Orthopedic Surgery, Nihon Koukan Hospital, 1-2-1 Koukandori, Kawasaki-ku, Kanagawa, Japan.
Department of Orthopedic Surgery, Showa University School of Medicine, 1-5-8 Hatanodai, Shinagawa-ku, Tokyo, Japan.
J Orthop Case Rep. 2022 Jul;12(7):18-21. doi: 10.13107/jocr.2022.v12.i07.2898.
Localized pigmented villonodular synovitis (PVNS) is a rare and benign condition of synovial tissue proliferation that affects the joints, tendon sheaths, and bursae. This case report is the first to describe a patient with a diagnosis of localized PVNS of the knee after presentation with bilateral and simultaneous onset of associated knee pain.
A 28-year-old Japanese woman presented to our hospital with a 1-year history of bilateral knee pain and right knee locking that started 1 month ago. Magnetic resonance imaging demonstrated a mass lesion in both the anterior compartment of the right knee and in the posterior compartments of the left knee. Arthroscopic resection of the lesions was performed, and the diagnosis of localized PVNS was made by pathological analysis. At the 6-month follow-up, no evidence of recurrence was noted.
This case report describes localized PVNS of the bilateral knee, which is extremely rare. PVNS is a disease requiring surgical resection and should not be overlooked. It should be treated with the possibility of bilateral occurrence in mind.
局限性色素沉着绒毛结节性滑膜炎（PVNS）是一种罕见的滑膜组织增生性良性疾病，可累及关节、腱鞘和滑囊。本病例报告首次描述了一名患者，在双侧同时出现相关膝关节疼痛后被诊断为膝关节局限性PVNS。
一名28岁的日本女性因双侧膝关节疼痛1年、右膝关节绞锁1个月前来我院就诊。磁共振成像显示右膝前侧间室和左膝后侧间室有肿块病变。对病变进行了关节镜下切除，并通过病理分析确诊为局限性PVNS。在6个月的随访中，未发现复发迹象。
本病例报告描述了双侧膝关节局限性PVNS，极为罕见。PVNS是一种需要手术切除的疾病，不应被忽视。应考虑到双侧发病的可能性进行治疗。
