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一名慢性肉芽肿病患者出现内脏利什曼病和附睾睾丸炎的罕见表现。

A rare presentation of visceral leishmaniasis and epididymo-orchitis in a patient with chronic granulomatous disease.

作者信息

Ashraf Talesh Shaghayegh, Mahmoudi Shima, Mohebali Mehdi, Mamishi Setareh

机构信息

Department of Infectious Diseases, Children's Medical Center Tehran University of Medical Sciences Tehran Iran.

Pediatric Infectious Disease Research Center Tehran University of Medical Sciences Tehran Iran.

出版信息

Clin Case Rep. 2023 May 31;11(6):e7426. doi: 10.1002/ccr3.7426. eCollection 2023 Jun.

DOI:10.1002/ccr3.7426
PMID:37273673
原文链接:https://pmc.ncbi.nlm.nih.gov/articles/PMC10233215/
Abstract

Visceral leishmaniasis (VL) has rarely been reported in patients with chronic granulomatous disease (CGD), despite the fact that they seem more susceptible to intracellular infection. We describe a rare presentation of VL and epididymo-orchitis in a patient with CGD, which has not been seen previously in the literature following inflammatory syndrome.

摘要

内脏利什曼病(VL)在慢性肉芽肿病(CGD)患者中鲜有报道,尽管事实上他们似乎更容易受到细胞内感染。我们描述了1例CGD患者罕见的VL合并附睾炎或睾丸炎表现,在炎性综合征之后,这种情况在文献中未曾见过。

https://cdn.ncbi.nlm.nih.gov/pmc/blobs/ed7c/10233215/973b3f0fcfaf/CCR3-11-e7426-g003.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/ed7c/10233215/5f7ba04de9be/CCR3-11-e7426-g001.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/ed7c/10233215/973b3f0fcfaf/CCR3-11-e7426-g003.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/ed7c/10233215/5f7ba04de9be/CCR3-11-e7426-g001.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/ed7c/10233215/973b3f0fcfaf/CCR3-11-e7426-g003.jpg

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本文引用的文献

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The Emergence of Co-Infection of Visceral Leishmaniasis in an Iranian Child with Chronic Granulomatous Disease: A Case Report.一名患有慢性肉芽肿病的伊朗儿童出现内脏利什曼病合并感染:病例报告
Iran J Parasitol. 2021 Jan-Mar;16(1):159-163. doi: 10.18502/ijpa.v16i1.5536.
2
Cutaneous, mucocutaneous and visceral leishmaniasis in Sweden from 1996-2016: a retrospective study of clinical characteristics, treatments and outcomes.1996-2016 年瑞典皮肤、黏膜和内脏利什曼病:临床特征、治疗和结局的回顾性研究。
BMC Infect Dis. 2018 Dec 7;18(1):632. doi: 10.1186/s12879-018-3539-1.
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Pediatric visceral leishmaniasis in northwest of Iran.
伊朗西北部的小儿内脏利什曼病
Medicine (Baltimore). 2016 Nov;95(44):e5261. doi: 10.1097/MD.0000000000005261.
4
Chronic granulomatous disease.慢性肉芽肿病
Br Med Bull. 2016 Jun;118(1):50-63. doi: 10.1093/bmb/ldw009. Epub 2016 Mar 16.
5
Infections associated with chronic granulomatous disease: linking genetics to phenotypic expression.慢性肉芽肿病相关感染:将遗传学与表型表达联系起来。
Expert Rev Anti Infect Ther. 2012 Aug;10(8):881-94. doi: 10.1586/eri.12.77.
6
Visceral leishmaniasis associated hemophagocytic syndrome in patients with chronic granulomatous disease.慢性肉芽肿病患者的内脏利什曼病相关噬血细胞综合征
Pediatr Infect Dis J. 2009 Aug;28(8):753-4. doi: 10.1097/INF.0b013e31819c6f3a.
7
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