Department of Education, California University of Science and Medicine, Colton, CA 92324, USA.
Nutrients. 2023 May 30;15(11):2551. doi: 10.3390/nu15112551.
Adult Refsum disease (ARD) is a rare peroxisomal biogenesis disorder inherited in an autosomal recessive fashion and is often characterized by retinitis pigmentosa, cerebellar ataxia, and polyneuropathy. Many patients with ARD require diet modification, psychosocial support, and various specialist visits to manage their symptoms. In this study, we explored the quality of life in individuals with ARD by analyzing retrospective survey data collected by the Coordination of Rare Diseases at Sanford (CoRDS) Registry and Global Defeat Adult Refsum Everywhere (DARE) Foundation. Statistical tests used were frequencies, mean, and median. There were 32 respondents, ranging between 11 and 32 responses for each question. The mean age at diagnosis was 35.5 ± 14.5 years (range 6-64) with 36.4% male and 63.6% female respondents. The average age for retinitis pigmentosa diagnosis was 22.8 ± 15.7 years (range 2-61). Dieticians were the most frequently seen (41.7%) for management of low-phytanic-acid diets. Most participants exercise at least once per week (92.5%). Depression symptoms were reported in 86.2% of the participants. Early diagnosis of ARD is important for managing symptoms and preventing progression of visual impairment due to phytanic acid buildup. Interdisciplinary approach should be used for patients to address physical and psychosocial impairments of ARD.
成人 Refsum 病(ARD)是一种罕见的过氧化物酶体生物发生障碍,呈常染色体隐性遗传,常表现为视网膜色素变性、小脑共济失调和多发性神经病。许多 ARD 患者需要通过饮食调整、社会心理支持和各种专科就诊来控制症状。在这项研究中,我们通过分析 Sanford 罕见疾病协调中心(CoRDS)登记处和全球战胜成人 Refsum 病基金会(DARE)收集的回顾性调查数据,探讨了 ARD 患者的生活质量。使用的统计检验方法是频率、均值和中位数。共有 32 名受访者,每个问题的回答范围在 11 到 32 个之间。诊断时的平均年龄为 35.5±14.5 岁(范围 6-64 岁),男性占 36.4%,女性占 63.6%。视网膜色素变性的平均诊断年龄为 22.8±15.7 岁(范围 2-61 岁)。营养师是管理低植烷酸饮食时最常就诊的科室(41.7%)。大多数参与者每周至少锻炼一次(92.5%)。86.2%的参与者报告有抑郁症状。早期诊断 ARD 对于控制症状和预防由于植烷酸堆积导致的视力损害进展非常重要。应采用多学科方法来解决 ARD 的身体和社会心理障碍。