Institute for Translational Medicine, Medical School, University of Pécs, Pécs, Hungary.
Division of Gastroenterology, Medical Department II, University of Leipzig Medical Center, Leipzig, Germany.
Pancreatology. 2023 Aug;23(5):481-490. doi: 10.1016/j.pan.2023.05.013. Epub 2023 May 29.
Chymotrypsin C (CTRC) is a digestive serine protease produced by the pancreas that regulates intrapancreatic trypsin activity and provides a defensive mechanism against chronic pancreatitis (CP). CTRC exerts its protective effect by promoting degradation of trypsinogen, the precursor to trypsin. Loss-of-function missense and microdeletion variants of CTRC are found in around 4% of CP cases and increase disease risk by approximately 3-7-fold. In addition, a commonly occurring synonymous CTRC variant c.180C>T (p.Gly60=) was reported to increase CP risk in various cohorts but a global analysis of its impact has been lacking. Here, we analyzed the frequency and effect size of variant c.180C>T in Hungarian and pan-European cohorts, and performed meta-analysis of the new and published genetic association data. When allele frequency was considered, meta-analysis revealed an overall frequency of 14.2% in patients and 8.7% in controls (allelic odds ratio (OR) 2.18, 95% confidence interval (CI) 1.72-2.75). When genotypes were examined, c.180TT homozygosity was observed in 3.9% of CP patients and in 1.2% of controls, and c.180CT heterozygosity was present in 22.9% of CP patients and in 15.5% of controls. Relative to the c.180CC genotype, the genotypic OR values were 5.29 (95% CI 2.63-10.64), and 1.94 (95% CI 1.57-2.38), respectively, indicating stronger CP risk in homozygous carriers. Finally, we obtained preliminary evidence that the variant is associated with reduced CTRC mRNA levels in the pancreas. Taken together, the results indicate that CTRC variant c.180C>T is a clinically relevant risk factor, and should be considered when genetic etiology of CP is investigated.
糜蛋白酶 C (CTRC) 是一种由胰腺产生的消化性丝氨酸蛋白酶,可调节胰内胰蛋白酶的活性,并提供一种防御机制以抵抗慢性胰腺炎 (CP)。CTRC 通过促进胰蛋白酶原(胰蛋白酶的前体)的降解来发挥其保护作用。CTRC 的失活功能错义突变和微缺失变体在大约 4%的 CP 病例中发现,并使疾病风险增加约 3-7 倍。此外,据报道,一种常见的同义 CTRC 变体 c.180C>T (p.Gly60=) 会增加各种队列中的 CP 风险,但缺乏对其影响的全球分析。在这里,我们分析了匈牙利和泛欧队列中变体 c.180C>T 的频率和效应大小,并对新的和已发表的遗传关联数据进行了荟萃分析。当考虑等位基因频率时,荟萃分析显示患者中的总体频率为 14.2%,对照组为 8.7%(等位基因优势比 (OR) 2.18,95%置信区间 (CI) 1.72-2.75)。当检查基因型时,c.180TT 纯合子在 3.9%的 CP 患者和 1.2%的对照组中观察到,c.180CT 杂合子在 22.9%的 CP 患者和 15.5%的对照组中存在。与 c.180CC 基因型相比,基因型 OR 值分别为 5.29 (95% CI 2.63-10.64) 和 1.94 (95% CI 1.57-2.38),表明纯合子携带者的 CP 风险更高。最后,我们初步得到证据表明该变体与胰腺中 CTRC mRNA 水平降低有关。综上所述,结果表明,CTRC 变体 c.180C>T 是一个具有临床意义的风险因素,在研究 CP 的遗传病因学时应考虑该变体。