Pharmacokinetic, Nanotechnology and Gene Therapy Group (PharmaNanoGene), Faculty of Pharmacy, Centro de Investigación Lascaray Ikergunea, University of the Basque Country, UPV/EHU, Paseo de la Universidad 7, Vitoria-Gasteiz, 01006, Spain.
Bioaraba, Microbiology, Infectious Disease, Antimicrobial Agents and Gene Therapy, Vitoria-Gasteiz, 01006, Spain.
Drug Deliv Transl Res. 2024 Oct;14(10):2615-2628. doi: 10.1007/s13346-024-01583-0. Epub 2024 Apr 8.
Fabry disease (FD) results from a lack of activity of the lysosomal enzyme α-Galactosidase A (α-Gal A), leading to the accumulation of glycosphingolipids in several different cell types. Protein supplementation by pDNA or mRNA delivery presents a promising strategy to tackle the underlying genetic defect in FD. Protein-coding nucleic acids in FD can be either delivered to the most affected sites by the disease, including heart, kidney and brain, or to specialized organs that can act as a production factory of the enzyme, such as the liver. Lipid-based systems are currently at the top of the ranking of non-viral nucleic acid delivery systems, and their versatility allows the linking to the surface of a wide range of molecules to control their biodistribution after intravenous administration. This systematic review follows the Preferred Reporting Items for Systematic Reviews and Meta-Analysis (PRISMA) statement guidelines and provides an overview and discussion of the targeting ligands that have been employed so far to actively vectorize intravenously administered non-viral vectors based on lipid carriers to clinically relevant organs in the treatment of FD, for protein-coding nucleic acid (pDNA and mRNA) supplementation. Among the thirty-two studies included, the majority focus on targeting the liver and brain. The targeting of the heart has been reported to a lesser degree, whereas no articles addressing kidney-targeting have been recorded. Although a great effort has been made to develop organ-specific nucleic acid delivery systems, the design of active-targeted carriers with high quality, good clinical translation, and large-scale manufacturing capacity is still challenging.
法布里病(FD)是由于溶酶体酶α-半乳糖苷酶 A(α-Gal A)缺乏活性,导致几种不同细胞类型中的糖脂积累而引起的。通过 pDNA 或 mRNA 递送来补充蛋白质是一种有前途的策略,可以解决 FD 中的潜在遗传缺陷。FD 中的蛋白质编码核酸可以通过疾病(包括心脏、肾脏和大脑)最受影响的部位或可以作为酶的生产工厂的专门器官(如肝脏)来递送到。基于脂质的系统目前在非病毒核酸递送系统的排名中名列前茅,其多功能性允许与广泛的分子表面连接,以控制其在静脉给药后的生物分布。本系统评价遵循系统评价和荟萃分析(PRISMA)报告标准的指导原则,并概述和讨论了迄今为止已用于主动静脉内递送至临床相关器官的基于脂质载体的非病毒载体的靶向配体,用于 FD 的蛋白质编码核酸(pDNA 和 mRNA)补充。在包括的三十二项研究中,大多数研究集中在靶向肝脏和大脑。心脏的靶向性报道较少,而没有记录到针对肾脏的靶向性文章。尽管为开发器官特异性核酸递送系统做出了巨大努力,但设计具有高质量、良好临床转化和大规模制造能力的主动靶向载体仍然具有挑战性。