Suppr超能文献

二尖瓣环干酪样钙化:心脏的钙化牙膏

Caseous Calcification of the Mitral Annulus: Calcified Toothpaste of the Heart.

作者信息

Jorgenson Kyla M, McMullen Phillip D, Goldman Bruce I, Jacob-Leonce Marisa

机构信息

From the University of Rochester Medical Center, Rochester, NY.

出版信息

Am J Forensic Med Pathol. 2025 Mar 1;46(1):59-63. doi: 10.1097/PAF.0000000000000971. Epub 2024 Jul 18.

Abstract

Caseous calcification of the mitral annulus (CCMA) is a rare variant of mitral annular calcification (MAC) usually described as an antemortem finding. We report a case of sudden cardiac arrest in a 39-year-old male with end-stage renal disease undergoing hemodialysis with a history of Fabry disease by kidney biopsy. Autopsy revealed significant circumferential annular calcification in both mitral and aortic valves with a caseous gross appearance. Histologically, these areas consisted of amorphous basophilic material accompanied by a surrounding granulomatous-appearing infiltrate. Von Kossa staining on non-decalcified tissue revealed strong positive staining, confirming CCMA diagnosis. While identifiable, the atrioventricular node was displaced and distorted by caseous deposits. Toluidine blue staining of myocardium showed osmophilic accumulations, and electron microscopy (EM) showed myeloid/zebra bodies, consistent with Fabry disease. We posit that Fabry disease leads to end-stage kidney disease, altering calcium phosphate metabolism, a proposed mechanism for CCMA. This case highlights the multifactorial nature of sudden cardiac death in decedents with various structural cardiac changes and potential renal-disease-induced electrolyte imbalances. We aim to bring awareness to this rare entity, its potential role in a sudden cardiac death, and to highlight the need to use non-decalcified tissue when staining for calcium to establish the diagnosis.

摘要

二尖瓣环干酪样钙化(CCMA)是二尖瓣环钙化(MAC)的一种罕见变异形式,通常被描述为生前发现的病变。我们报告一例39岁男性终末期肾病患者,正在接受血液透析,肾活检确诊为法布里病,该患者发生心脏骤停。尸检显示二尖瓣和主动脉瓣均有显著的环形钙化,外观呈干酪样。组织学检查发现,这些区域由无定形嗜碱性物质组成,并伴有周围肉芽肿样浸润。对未脱钙组织进行冯·科萨染色显示强阳性,确诊为CCMA。虽然房室结可辨认,但被干酪样沉积物移位和扭曲。心肌甲苯胺蓝染色显示嗜锇性积聚,电子显微镜(EM)显示髓样/斑马小体,符合法布里病表现。我们推测法布里病导致终末期肾病,改变磷酸钙代谢,这是CCMA的一种可能机制。该病例突出了具有各种心脏结构改变和潜在肾病引起的电解质失衡的死者心脏性猝死的多因素性质。我们旨在提高对这种罕见疾病的认识,其在心脏性猝死中的潜在作用,并强调在进行钙染色以确立诊断时使用未脱钙组织的必要性。

https://cdn.ncbi.nlm.nih.gov/pmc/blobs/ea7f/11801426/936e845a275c/fmp-46-59-g001.jpg

文献AI研究员

20分钟写一篇综述,助力文献阅读效率提升50倍。

立即体验

用中文搜PubMed

大模型驱动的PubMed中文搜索引擎

马上搜索

文档翻译

学术文献翻译模型,支持多种主流文档格式。

立即体验