Haddad Eliot N, Kumar Pranav, Shearn-Nance Galen, Kharal G Abbas, Dhawan Andrew
From the Cleveland Clinic Lerner College of Medicine (E.N.H., A.D., G.A.K.); School of Medicine (P.K., G.S.-N.), Case Western Reserve University; and Neurological Institute (A.D., G.A.K.), Cleveland Clinic, OH.
Neurol Genet. 2024 Aug 21;10(5):e200182. doi: 10.1212/NXG.0000000000200182. eCollection 2024 Oct.
Genetic arteriopathies leading to stroke in adults constitute a diverse group of cerebrovascular disorders with distinct etiologies, pathophysiologic mechanisms, and clinical presentations. As imaging modalities better delineate subtle changes in cerebral vasculature and access to genetic testing increases, the detection rate for these conditions is expected to rise, particularly among young adults with idiopathic cerebral arteriopathy and stroke. Adults with stroke in the setting of a genetic cerebral arteriopathy often present with few traditional stroke risk factors and, in certain cases, have characteristic clinical features, cerebrovascular imaging findings, and often concurrent systemic vasculopathy, such as aortopathy, which are important to recognize. Given that there are over 50 recognized genetic cerebral arteriopathies that can cause ischemic and hemorrhagic stroke in young adults, it can be a significant diagnostic challenge for the practicing neurologist when faced with a genetic cerebral arteriopathy, because clinical algorithms for a systematic approach to genetic cerebral arteriopathies are lacking. In this review, we present a phenotype-driven, clinically oriented algorithm to guide the diagnostic workup when suspecting a genetic cerebral arteriopathy in an adult patient while highlighting the genetic basis of each disease, molecular mechanisms, clinical manifestations, diagnostic approaches, and emerging therapeutic strategies. Moreover, given the lack of widely available gene panels for diagnostic germline testing for genetic cerebral arteriopathies, we propose key genes to be tested and focused on in each clinical scenario, to better decipher the underlying diagnosis in these rare conditions.
导致成人中风的遗传性动脉病是一组多样的脑血管疾病,具有不同的病因、病理生理机制和临床表现。随着成像方式能更好地描绘脑血管的细微变化以及基因检测的可及性增加,预计这些疾病的检出率将会上升,尤其是在患有特发性脑动脉病和中风的年轻人中。患有遗传性脑动脉病性中风的成年人通常很少有传统的中风危险因素,在某些情况下,具有特征性的临床特征、脑血管成像表现,并且常常并发系统性血管病,如主动脉病变,这些都很重要,需要识别。鉴于有超过50种已被认可的遗传性脑动脉病可导致年轻人缺血性和出血性中风,对于执业神经科医生来说,面对遗传性脑动脉病时可能是一项重大的诊断挑战,因为缺乏用于系统性诊断遗传性脑动脉病的临床算法。在本综述中,我们提出一种以表型为驱动、以临床为导向的算法,以指导在怀疑成年患者患有遗传性脑动脉病时的诊断检查,同时突出每种疾病的遗传基础、分子机制、临床表现、诊断方法和新兴治疗策略。此外,鉴于缺乏广泛可用的用于遗传性脑动脉病诊断性种系检测的基因panel,我们提出在每种临床情况下要检测和关注的关键基因,以便更好地解读这些罕见疾病的潜在诊断。