Yorita Kenji, Miyazaki Katsushi, Hisaoka Masanori, Nakatani Kimiko
Diagnostic Pathology, Japanese Red Cross Kochi Hospital, Kochi, JPN.
Otolaryngology, Japanese Red Cross Kochi Hospital, Kochi, JPN.
Cureus. 2024 Aug 29;16(8):e68079. doi: 10.7759/cureus.68079. eCollection 2024 Aug.
A 17-year-old Japanese male presented with a nasal polyp and neck lymphadenopathy. He was referred to our hospital for diagnosis and treatment of neck lymphadenopathy. Grossly, a whitish pedunculated nasal polyp was observed on the right side of the nasal septum. Computed tomography confirmed the presence of a nasal polyp and two nodular lesions in the right maxillary sinus. All three lesions showed no contrast enhancement. Clinical examination revealed neck lymphadenopathy, suggestive of Kikuchi disease. The nasal polyp was resected, and pathological examination revealed an inflammatory nasal polyp with benign lymphangioendothelioma, also known as acquired progressive lymphangioma. The right maxillary sinus nodules were followed up. The nasal occurrence of benign lymphangioendothelioma is markedly unusual, as the lesion typically occurs in the skin. To the best of our knowledge, this is the first reported case of nasal benign lymphangioendothelioma in our review of the PubMed database.
一名17岁日本男性因鼻息肉和颈部淋巴结病就诊。他因颈部淋巴结病被转诊至我院进行诊断和治疗。肉眼可见，在鼻中隔右侧有一个带蒂的白色鼻息肉。计算机断层扫描证实存在鼻息肉以及右侧上颌窦内的两个结节性病变。所有三个病变均无强化。临床检查发现颈部淋巴结病，提示为菊池病。切除鼻息肉后，病理检查显示为伴有良性淋巴管内皮瘤（也称为获得性进行性淋巴管瘤）的炎性鼻息肉。对右侧上颌窦结节进行了随访。良性淋巴管内皮瘤发生于鼻腔极为罕见，因为该病变通常发生于皮肤。据我们所知，在检索PubMed数据库时，这是首例报道的鼻腔良性淋巴管内皮瘤病例。
