Feher Jan Kuschick, Marin-Castañeda Luis A, Juárez-Tovar Fernando S, Carrillo-Mezo Roger, Rosas Gabriela, Tena-Suck Martha Lilia, Fleury Agnès
Peripheral Unit for the Study of Neuroinflammation, Instituto de Investigaciones Biomédicas, Universidad Nacional Autónoma de México, Mexico City, Mexico.
Neurophysiology Department, Instituto Nacional de Neurología y Neurocirugía "Manuel Velasco Suárez", Mexico City, Mexico.
Case Rep Neurol Med. 2024 Oct 25;2024:9673413. doi: 10.1155/2024/9673413. eCollection 2024.
Neurenteric cysts (NECs) are rare congenital, benign lesions of the central nervous system (CNS), predominantly located within the spinal cord. However, they may also occur less frequently within the brainstem, fourth ventricle, or cerebellopontine angle (CPA). Originating from anomalous interactions between embryonic layers, NECs are recognized for their potential to compress adjacent structures. We report a unique case of disseminated NECs exhibiting few to absent symptoms, which represents an unusual presentation of this disease, with only six similar reports in the literature. A 22-year-old female presented to our institute with chronic headaches resistant to nonsteroidal anti-inflammatory drugs (NSAIDs). Initially treated for intracranial hypertension (ICH) secondary to a cyst in the quadrigeminal cistern at the age of 17 via neuroendoscopic surgery and subsequent ventriculoperitoneal shunting, she experienced transient relief. However, follow-up at 22 years of age revealed multiple cysts in the basal and spinal cisterns, with MRI findings suggestive of neurocysticercosis. Despite treatment with albendazole and corticosteroids, subsequent MRIs showed no change in the size or number of the cysts. Six years later, symptoms had worsened, previously identified cysts had grown, and the detection of new cysts prompted surgical intervention. Histopathological examination confirmed the presence of NECs. This case highlights the diagnostic challenges posed by NECs, especially in regions endemic for neurocysticercosis, where clinical and radiological findings may initially suggest this condition. It underscores the importance of considering NECs in the differential diagnosis of cystic lesions in the CNS, even in the absence of typical symptoms of spinal cord compression. The recurrence and spread of NECs post-treatment demand a comprehensive management approach, encompassing surgical intervention and close monitoring.
神经肠囊肿(NECs)是中枢神经系统(CNS)罕见的先天性良性病变,主要位于脊髓内。然而,它们也较少见地发生于脑干、第四脑室或桥小脑角(CPA)。NECs起源于胚胎层之间的异常相互作用,因其有压迫相邻结构的可能性而被认识。我们报告了一例独特的播散性NECs病例,该病例症状轻微或无明显症状,这是该疾病的一种不寻常表现,文献中仅有六例类似报道。一名22岁女性因对非甾体抗炎药(NSAIDs)治疗无效的慢性头痛前来我院就诊。她17岁时因四叠体池囊肿继发颅内高压(ICH),最初接受了神经内镜手术及随后的脑室腹腔分流术,术后有短暂缓解。然而,22岁时的随访发现基底池和脊髓池有多个囊肿,MRI表现提示神经囊尾蚴病。尽管使用了阿苯达唑和皮质类固醇治疗,但后续MRI显示囊肿大小和数量均无变化。六年后,症状加重,先前发现的囊肿增大,新囊肿的发现促使进行手术干预。组织病理学检查证实为NECs。该病例突出了NECs带来的诊断挑战,尤其是在神经囊尾蚴病流行地区,临床和影像学表现最初可能提示为这种疾病。它强调了在中枢神经系统囊性病变的鉴别诊断中考虑NECs的重要性,即使没有脊髓压迫的典型症状。NECs治疗后的复发和播散需要一种综合管理方法,包括手术干预和密切监测。