Watanabe Hirofumi, Enda Kodai, Fujishima Fumiyoshi, Shirota Hidekazu, Ninomiya Masashi, Yamazaki Tetsuro, Sasano Hironobu, Suzuki Takashi
Department of Pathology, Tohoku University Hospital, Sendai, Miyagi, Japan.
Department of Medical Oncology, Tohoku University Hospital, Sendai, Miyagi, Japan.
Med Mol Morphol. 2025 Mar;58(1):83-86. doi: 10.1007/s00795-024-00408-w. Epub 2024 Nov 10.
This report presents a rare case of a 45-year-old man diagnosed with a primary hepatic alpha-fetoprotein-producing neuroendocrine neoplasm, a condition rarely reported in the literature. The patient presented with initial symptoms of back and epigastric pain, after which multiple liver lesions were discovered on contrast-enhanced computed tomography, suggesting intrahepatic cholangiocarcinoma. Histopathological and immunohistochemical analyses confirmed the diagnosis of alpha-fetoprotein-producing neuroendocrine neoplasm that was further supported by genetic testing, which revealed FGFR2 and TP53 mutations commonly encountered in intrahepatic cholangiocarcinoma. Despite receiving various chemotherapeutic regimens, the patient exhibited a progressive disease. This case underscores the importance of accurate differential diagnosis from hepatocellular carcinoma and intrahepatic cholangiocarcinoma due to differences in treatment approaches and prognoses and highlights the necessity for increased awareness of AFP-producing primary hepatic neuroendocrine neoplasms among clinicians and pathologists. It emphasizes the significance of comprehensive histopathological evaluation, immunohistochemical profiling, and genetic analysis for precise diagnosis and tailored therapeutic strategies. Further research is warranted to elucidate the molecular mechanisms underlying this rare liver tumor subtype and develop targeted treatments.
本报告介绍了一例罕见病例,一名45岁男性被诊断为原发性肝产甲胎蛋白神经内分泌肿瘤,这一病症在文献中鲜有报道。患者最初表现为背部和上腹部疼痛,之后在增强计算机断层扫描中发现多个肝脏病变,提示肝内胆管癌。组织病理学和免疫组织化学分析确诊为产甲胎蛋白神经内分泌肿瘤,基因检测进一步支持了这一诊断,检测发现了肝内胆管癌中常见的FGFR2和TP53突变。尽管接受了各种化疗方案,患者病情仍进展。该病例强调了由于治疗方法和预后不同,准确鉴别诊断肝细胞癌和肝内胆管癌的重要性,并突出了临床医生和病理学家提高对产甲胎蛋白原发性肝神经内分泌肿瘤认识的必要性。它强调了全面的组织病理学评估、免疫组织化学分析和基因分析对于精确诊断和制定个性化治疗策略的重要性。有必要进行进一步研究以阐明这种罕见肝肿瘤亚型的分子机制并开发靶向治疗方法。