Wilson Michele, Castaman Giancarlo, Thomas Will, Millar Carolyn, Escolar Ginés, Miesbach Wolfgang, McDade Cheryl, Tomic Radovan, Yan Songkai
RTI Health Solutions, Research Triangle Park, NC.
Center for Bleeding Disorders and Coagulation, Careggi University Hospital, Florence, Italy.
Blood Adv. 2025 Mar 25;9(6):1312-1319. doi: 10.1182/bloodadvances.2024014376.
von Willebrand factor (VWF) concentrates may be required for on-demand treatment (ODT) or long-term prophylaxis (LTP) in von Willebrand disease (VWD). This study assesses the cost-effectiveness of LTP compared with ODT in patients with VWD treated with Voncento in the United Kingdom. A Markov structure was developed to estimate the quality-adjusted life years (QALYs) and costs of VWD treatment over a lifetime horizon. Treatment options included ODT or LTP. For both options, we assumed plasma-derived VWF/factor VIII 2.4:1 (Voncento) as the VWF product used. Clinical parameters were obtained from published literature and Voncento's summary characteristics. Utility weights were obtained from published literature. Costs (in 2021 GBP [£]) and outcomes were discounted annually by 3.5%. Sensitivity analyses were conducted. Three baseline annual bleed rate (ABR) scenarios (11, 26.5, and 39.6) were considered. In the base-case analyses, Voncento LTP resulted in lower costs (-£831 206) and greater QALYs (6.14) vs ODT. Savings were primarily due to reductions in product use required (-£529 571) and bleed-related other medical costs (-£301 352). Compared with ODT, LTP also resulted in 322.52 fewer major bleeds and 515.68 fewer minor bleeds over a lifetime horizon. Probabilistic sensitivity analyses showed dominance in 96.12% of simulations and cost-effectiveness in 97.68% of simulations. For the 39.6 ABR scenario also, LTP was dominant compared with ODT. Results suggest that Voncento LTP is more effective and cost saving than ODT in the United Kingdom for patients with VWD with higher ABR. Prophylaxis for patients with frequent bleeds is likely to be a cost-saving and effective strategy.
在血管性血友病(VWD)中,按需治疗(ODT)或长期预防(LTP)可能需要使用血管性血友病因子(VWF)浓缩物。本研究评估了在英国接受Voncento治疗的VWD患者中,LTP与ODT相比的成本效益。构建了一个马尔可夫模型结构,以估计VWD患者一生治疗中的质量调整生命年(QALY)和成本。治疗方案包括ODT或LTP。对于这两种方案,我们假设使用血浆源性VWF/凝血因子VIII 2.4:1(Voncento)作为VWF产品。临床参数来自已发表的文献和Voncento的总结特征。效用权重来自已发表的文献。成本(以2021年英镑[£]计)和结果每年按3.5%进行贴现。进行了敏感性分析。考虑了三种基线年出血率(ABR)情景(11、26.5和39.6)。在基础病例分析中,与ODT相比,Voncento LTP导致成本降低(-831,206英镑)和QALY增加(6.14)。节省主要归因于所需产品使用量的减少(-529,571英镑)和与出血相关的其他医疗成本的降低(-301,352英镑)。与ODT相比,LTP在一生治疗期间还导致主要出血减少322.52次,轻微出血减少515.68次。概率敏感性分析显示,在96.12%的模拟中LTP占主导地位,在97.68%的模拟中具有成本效益。对于ABR为39.6的情景,与ODT相比,LTP也占主导地位。结果表明,在英国,对于ABR较高的VWD患者,Voncento LTP比ODT更有效且节省成本。对频繁出血患者进行预防可能是一种节省成本且有效的策略。