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一例分娩期间自发性纵隔气肿(哈曼综合征)的病例报告。

A Case Report of Spontaneous Pneumomediastinum (Hamman's Syndrome) During Labor.

作者信息

Barrera-Hoffmann Christopher, Mariaca-Ortíz Yadira, Rodríguez-Flota Mauro Alejandro, Cerda-García Paul Alejandro, Monares-Zepeda Enrique

机构信息

Critical Care Medicine, Instituto Mexicano del Seguro Social, Juarez, MEX.

Nephrology, Instituto Nacional de Cardiologia Ignacio Chávez, Mexico City, MEX.

出版信息

Cureus. 2024 Dec 18;16(12):e75944. doi: 10.7759/cureus.75944. eCollection 2024 Dec.

DOI:10.7759/cureus.75944
PMID:39835024
原文链接:https://pmc.ncbi.nlm.nih.gov/articles/PMC11742758/
Abstract

Hamman's syndrome is characterized by spontaneous pneumomediastinum triggered by Valsalva maneuvers and is an uncommon complication during labor and the postpartum period. It is typically benign and managed conservatively with oxygen therapy and analgesia. We present the clinical case of a 21-year-old primigravida who developed spontaneous pneumomediastinum during labor, manifesting with subcutaneous emphysema and dyspnea. It was documented by a chest X-ray and CT scan, and improved with conservative treatment. The patient was discharged without complications or recurrence. Hamman's syndrome is a rare condition, so recognizing it accurately is fundamental. This allows for timely treatment initiation, detection of complications, and exclusion of other pathologies, all of which affect patient prognosis.

摘要

哈曼综合征的特征是由瓦尔萨尔瓦动作引发的自发性纵隔气肿,是分娩和产后期间一种罕见的并发症。它通常为良性,采用氧疗和镇痛进行保守治疗。我们报告了一例21岁初产妇的临床病例,该患者在分娩期间发生自发性纵隔气肿,表现为皮下气肿和呼吸困难。通过胸部X线和CT扫描得以确诊,并经保守治疗后好转。患者出院时无并发症且未复发。哈曼综合征是一种罕见疾病,因此准确识别至关重要。这有助于及时开始治疗、发现并发症并排除其他病变,所有这些都会影响患者的预后。

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本文引用的文献

1
Pneumomediastinum and Pericardium During Labour: A Report on a Rare Postpartum Phenomenon.分娩期间的纵隔气肿和心包积气:一例罕见产后现象的报告
Cureus. 2023 Dec 20;15(12):e50850. doi: 10.7759/cureus.50850. eCollection 2023 Dec.
2
A Rare Complication during Vaginal Delivery, Hamman's Syndrome: A Case Report and Systematic Review of Case Reports.阴道分娩罕见并发症:哈曼综合征 1 例报告及病例报告系统评价。
Int J Environ Res Public Health. 2022 Apr 12;19(8):4618. doi: 10.3390/ijerph19084618.
3
Spontaneous primary pneumomediastinum: is it always benign?
自发性纵隔气肿:总是良性的吗?
J Med Case Rep. 2021 Mar 25;15(1):157. doi: 10.1186/s13256-021-02701-z.
4
Pneumomediastinum following spontaneous vaginal delivery: report of a rare phenomenon.自然阴道分娩后发生纵隔气肿:罕见现象报告
J Surg Case Rep. 2020 Jun 17;2020(6):rjaa076. doi: 10.1093/jscr/rjaa076. eCollection 2020 Jun.
5
Facial swelling and dysphonia during labour: a case of Hamman's syndrome.分娩期间面部肿胀和声音嘶哑:1例哈曼综合征病例。
BMJ Case Rep. 2019 Jun 26;12(6):e227489. doi: 10.1136/bcr-2018-227489.
6
Pregnancy-associated Spontaneous Pneumomediastinum: A Contemporary Review.妊娠相关自发性纵隔气肿:当代综述
Cureus. 2018 Oct 15;10(10):e3452. doi: 10.7759/cureus.3452.
7
Spontaneous Pneumomediastinum in Labor.分娩时自发性纵隔气肿
Case Rep Obstet Gynecol. 2017;2017:6235076. doi: 10.1155/2017/6235076. Epub 2017 Feb 21.
8
Clinical experience of spontaneous pneumomediastinum: diagnosis and treatment.自发性纵隔气肿的临床经验:诊断与治疗
J Thorac Dis. 2015 Oct;7(10):1817-24. doi: 10.3978/j.issn.2072-1439.2015.10.58.
9
Spontaneous pneumomediastinum: time for consensus.自发性纵隔气肿:达成共识的时候了。
N Am J Med Sci. 2013 Aug;5(8):460-4. doi: 10.4103/1947-2714.117296.
10
Spontaneous pneumomediastinum following normal labour.正常分娩后自发性纵隔气肿
BMJ Case Rep. 2011 Oct 20;2011:bcr0720114556. doi: 10.1136/bcr.07.2011.4556.